High Risk Neuroblastoma Study 1.8 of SIOP-Europe (SIOPEN)

NCT ID: NCT01704716

Last Updated: 2020-10-23

Study Results

Results pending

The study team has not published outcome measurements, participant flow, or safety data for this trial yet. Check back later for updates.

Basic Information

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Recruitment Status

RECRUITING

Clinical Phase

PHASE3

Total Enrollment

3300 participants

Study Classification

INTERVENTIONAL

Study Start Date

2002-02-28

Study Completion Date

2026-09-30

Brief Summary

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This is a randomized study of the European SIOP Neuroblastoma Group (SIOPEN) in high-risk neuroblastoma (stages 2, 3, 4 and 4s MYCN-amplified neuroblastoma, stage 4 MYCN non amplified \> 12 months at diagnosis).

The protocol consists of a rapid, dose intensive induction chemotherapy, peripheral blood stem cell harvest, attempted complete excision of the primary tumour, myeloablative therapy followed by peripheral blood stem cell rescue, radiotherapy to the site of the primary tumour and immunotherapy (R4 randomization - isotretinoin and ch14.18/CHO (Dinutuximab beta, Qarziba ®).), with or without s.c. aldesleukin (IL-2)). Patients diagnosed after the closure of R3 randomization will not be R4 randomized. For these patients the use of ch14.18/CHO antibody is recommended without scIL-2 as continuous infusion as standard of care outside of controlled trials. ch14.18/CHO received marketing authorization by EMA in May 2017 (Qarziba ®).

In the induction phase, all patients receive Rapid COJEC following the result of the R3 randomization which was closed on June 8th, 2017 after inclusion of 630 patients as planned.

Following induction treatment peripheral blood stem cell harvest (PBSCH) is performed and complete excision of the primary tumour will be attempted.

Patients with an inadequate metastatic response to allow BuMel MAT followed by PBSCR at the end of induction should receive 2 TVD (Topotecan, Vincristine, Doxorubicin) cycles.

After Rapid COJEC induction, localized patients will proceed to consolidation. Patients aged 12-18 months at diagnosis, with stage 4 neuroblastoma, no MYCN amplification and without segmental chromosomal alterations (SCAs) are thought to have a good prognosis and will stop treatment after induction therapy and surgery to the primary tumour.

Consolidation consists of BuMel MAT based on the results of the R1 randomization followed by peripheral blood stem cell rescue (PBSCR) and radiotherapy to the site of the primary tumour.

The R2 immunotherapy randomization using ch14.18/CHO as 8 hour infusion on 5 consecutive days ( total dose (100mg/m²) with or without aldesleukin (IL-2) alternated with isotretinoin (13-cis-RA) is closed.

The amended R4 immunotherapy randomization using ch14.18/CHO as continuous infusion (total dose 100mg/m² over 10 days) with or without aldesleukin (IL-2) alternated with isotretinoin (13-cis-RA) has accrued according to plan with results pending awaiting data maturity and DMC approval.

Detailed Description

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In this protocol the term high-risk neuroblastoma refers to children with either

* disseminated disease (INSS stage 4: about 40 to 50% of all neuroblastoma) over the age of one or
* INSS stage 2 and 3 disease with amplification of the MycN proto-oncogene Between 10% and 20% of children with stage 3 and occasional patients with stage 2 disease are characterized by amplification of the MycN gene in their tumours. This biological characteristic has clearly been shown to be associated with a greater risk of relapse and death from disease progression. These patients may benefit from very aggressive treatment and, based on this hypothesis, they are included in this protocol. Infants (\< 12 months at diagnosis) with MYCN amplified tumors are included.

Children with this type of presentation and age represent the largest neuroblastoma subgroup. Their prognosis remains poor in most cases and our ability to predict the clinical course and the outcome of the individual patient is modest.

Primary objectives:

R0 randomization: R0 was opened with the study activation in February 2002 and closed in November 2005. The randomized use of G-CSF during COJEC induction resulted in the recommendation of the prophylactic use of G-CSF to prevent episodes of febrile neutropenia (Ladenstein R, Valteau-Couanet D, Brock P, et al. Randomized Trial of prophylactic granulocyte colony-stimulating factor during rapid COJEC induction in pediatric patients with high-risk neuroblastoma: the European HR-NBL1/SIOPEN study. J Clin Oncol. 2010 Jul 20;3516-24).

R1 randomization: R1 was opened with the study activation in February 2002 and closed in 10/2010 following the results showing significant superiority of myeloablative therapy (MAT) with busulfan and melphalan over continuous infusion of carboplatin, etoposide and melphalan (CEM). BuMel is now the standard MAT (Ladenstein R, Pötschger U, Pearson ADJ, et al. Busulfan and melphalan versus carboplatin, etoposide, and melphalan as high-dose chemotherapy for high-risk neuroblastoma (HR-NBL1/SIOPEN): an international, randomized, multi-arm, open-label, phase 3 trial. Lancet Oncol. 2017 Apr;500-14).

R2 randomization: R2 was activated in November 2006 (13-cis retinoic acid +/- chimeric ch14.18/CHO antibody), modified in July 2009 and suspended in August 2013. R2 randomization tested the hypothesis that immunotherapy with ch14.18/CHO and subcutaneous aldesleukin (IL-2, Proleukin®), following MAT and autologous stem cell transplantation, in addition to differentiation therapy with 13-cis retinoic acid, will improve 3-year EFS in patients with high-risk neuroblastoma (ASCO 2016: Ladenstein R, et al J Clin Oncol 34, 2016 (suppl; abstr 10500)).

R3 randomization: R3 was opened in June 2011 and tests the hypothesis that modified N7 induction regimen will improve the metastatic response rates or event free survival (EFS) as compared to Rapid COJEC. As of June 8th, 2017 R3 randomization reached the target of 630 randomized patients as planned. There was no difference in event free survival rate between both regimens (Rapid COJEC and modified N7), but modified N7 had a significantly higher grade 3 and 4 toxicity profile. Therefore, Rapid COJEC is maintained as the SIOPEN standard induction treatment with G-CSF support based on the results of the R0 randomization open from 2002 top 2005 This change has been implemented in amendment 8 of the protocol.

R4 randomization: R4 was activated in April 2014. The SIOPEN long term infusion (LTI) ch14.18/CHO trial successfully lowered the toxicity profile by prolonging the infusion time of the same total ch14.18/CHO antibody dose of 100 mg/m² to 10 days of continuous infusion in relapsed /refractory patients. Hence the HRNBL1/SIOPEN study committee wished to implement this more favorable immunotherapy dosing schedule for the time till the induction question R3 was answered and the HRNBL1/SIOPEN trial may be closed. Considering the high R2 dropout rate of patients unable to receive all immunotherapy cycles in the IL-2 s.c. combination treatment arm and not observing this effect in the current SIOPEN LTI trial, it is suggested to address the IL-2sc dose in the new R4. Therefore the potential synergistic effect of sc IL-2 will be addressed again with 50% of the original s.c. IL-2 dose. The IL-2sc dose will hence be reduced to 3 x 106 IU IL-2/m2/day s.c. in the HR-NBL1/SIOPEN R4 amendment instead of 6 x 106 IU IL-2/m2/day s.c as used in the SIOPEN LTI trial. In the second week of each IT course s.c.IL-2 will be given on days 2, 4, 6, 8, 10 in parallel to the ch14.18/CHO ctn infusion and not during the first 5 days in week 2 as scheduled in the SIOPEN LTI trial. R4 randomization is closed for patients diagnosed after June 8th, 2017, the closure date of R3 randomization. For these patients the use of ch14.18/CHO antibody is recommended without scIL-2 as continuous infusion (total dose 100 mg/m² over 10 days) as standard of care outside of controlled trials without scIL-2. The ch14.18/CHO monoclonal antibody received marketing authorization by EMA in May 2017 (dinutuximab beta, Qarziba®).

Conditions

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Neuroblastoma

Study Design

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Allocation Method

NON_RANDOMIZED

Intervention Model

PARALLEL

Primary Study Purpose

TREATMENT

Blinding Strategy

NONE

Study Groups

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R0: COJEC plus G-CSF

Patients randomised to G-CSF during induction treatment (Rapid COJEC) received a single daily subcutaneous injection of 5 microgram/kg/day G-CSF (filgrastim) beginning 24 hours after the last chemotherapy dose.

Group Type EXPERIMENTAL

Carboplatin

Intervention Type DRUG

Carboplatin is given during induction Treatment (R3 randomisation: Rapid COJEC arm)

Etoposide

Intervention Type DRUG

Etoposide is given during Induction Treatment (both R3 randomisation arms)

Cisplatin

Intervention Type DRUG

Cisplatin is given during Induction Treatment (both R3 randomisation arms)

Cyclophosphamide

Intervention Type DRUG

Cyclophosphamid is given during Induction Treatment (both R3 randomisation arms)

G-CSF

Intervention Type DRUG

G-CSF is given during Induction Treatment

R0: COJEC

Induction treatment (COJEC) without filgrastim Patients randomised to Rapid COJEC alone will receive induction Treatment without G-CSF

Group Type ACTIVE_COMPARATOR

Vincristine

Intervention Type DRUG

given during Rapid COJEC and modified N7 therapy

Carboplatin

Intervention Type DRUG

Carboplatin is given during induction Treatment (R3 randomisation: Rapid COJEC arm)

Etoposide

Intervention Type DRUG

Etoposide is given during Induction Treatment (both R3 randomisation arms)

Cisplatin

Intervention Type DRUG

Cisplatin is given during Induction Treatment (both R3 randomisation arms)

Cyclophosphamide

Intervention Type DRUG

Cyclophosphamid is given during Induction Treatment (both R3 randomisation arms)

R1: BuMel MAT

The BuMel MAT regimen consists of oral administration of busulphan and the short i.v. infusion of melphalan.

In July 2007 (amendment 3) oral busulfan was changed to i.v. Busulfan (Busilvex)

Group Type ACTIVE_COMPARATOR

Busulfan

Intervention Type DRUG

In case i.v. busulfan is not available, the use of oral busulfan is permitted, although not recommended.

Melphalan

Intervention Type DRUG

Melphalan is given during MAT treatment

R1: CEM MAT

The CEM MAT regimen uses three drugs: the dose of Carboplatin must be based on renal function with a target area under the concentration versus time curve (AUC) of 16.4 mg/ml.min, etoposide 350 mg/m2/course and melphalan 210 mg/m2/course

Group Type EXPERIMENTAL

Carboplatin

Intervention Type DRUG

Carboplatin is given during induction Treatment (R3 randomisation: Rapid COJEC arm)

Etoposide

Intervention Type DRUG

Etoposide is given during Induction Treatment (both R3 randomisation arms)

Melphalan

Intervention Type DRUG

Melphalan is given during MAT treatment

R2: ch14.18/CHO

ch14.18/CHO is given at a dose of 20 mg/m2/day over five days every four weeks for five courses

Group Type ACTIVE_COMPARATOR

ch14.18/CHO

Intervention Type DRUG

ch14.18/CHO antibody is given during MRD treatment

R2: ch14.18/CHO plus Aldesleukin

Patients randomised to receive ch14.18/CHO plus Aldesleukin

Group Type EXPERIMENTAL

Aldesleukin

Intervention Type DRUG

Aldesleukin is given during MRD Treatment for patients randomised to the arm with IL-2

ch14.18/CHO

Intervention Type DRUG

ch14.18/CHO antibody is given during MRD treatment

R3: COJEC Induction

Rapid COJEC induction treatment is applied over ten weeks; three different courses are given every ten days:

Course A (given on days 0 and 40): vincristine, carboplatin, and etoposide Course B (given on days 10, 30, 50, and 70): vincristine and cisplatin Course C (given on days 20 and 60): vincristine, etoposide, and cyclophosphamide

Group Type ACTIVE_COMPARATOR

Vincristine

Intervention Type DRUG

given during Rapid COJEC and modified N7 therapy

Carboplatin

Intervention Type DRUG

Carboplatin is given during induction Treatment (R3 randomisation: Rapid COJEC arm)

Etoposide

Intervention Type DRUG

Etoposide is given during Induction Treatment (both R3 randomisation arms)

Cisplatin

Intervention Type DRUG

Cisplatin is given during Induction Treatment (both R3 randomisation arms)

Cyclophosphamide

Intervention Type DRUG

Cyclophosphamid is given during Induction Treatment (both R3 randomisation arms)

R3: Modified N7

The modified N7 induction is a dose intense induction chemotherapy regimen including two putatively non cross-resistent drug combinations: high-dose cyclophosphamide plus doxorubicin/vincristine (CAV) and high-dose cisplatin/etoposide (P/E).

Group Type EXPERIMENTAL

Vincristine

Intervention Type DRUG

given during Rapid COJEC and modified N7 therapy

Etoposide

Intervention Type DRUG

Etoposide is given during Induction Treatment (both R3 randomisation arms)

Cisplatin

Intervention Type DRUG

Cisplatin is given during Induction Treatment (both R3 randomisation arms)

Cyclophosphamide

Intervention Type DRUG

Cyclophosphamid is given during Induction Treatment (both R3 randomisation arms)

Doxorubicin

Intervention Type DRUG

Doxorubicin is given during Induction Treatment (R3 arm modified N7)

R4: cnt inf ch14.18/CHO

ch14.18/CHO is given as continuous Infusion over 10 days at a cumulative dose of 100mg/m2. Patients receive 5 cycles of ch14.18/CHO

Group Type ACTIVE_COMPARATOR

ch14.18/CHO

Intervention Type DRUG

ch14.18/CHO antibody is given during MRD treatment

R4: cnt inf ch14.18/CHO plus Aldesleukin

ch14.18/CHO is given as continuous Infusion over 10 days at a cumulative dose of 100mg/m2. Patients receive 5 cycles of ch14.18/CHO.

In addition, Aldesleukin is given at a dose of 3 x 10e6 on days 1 to 5 and on days 9, 11, 13, 15, and 17 during ch14.18/CHO infusion

Group Type EXPERIMENTAL

Aldesleukin

Intervention Type DRUG

Aldesleukin is given during MRD Treatment for patients randomised to the arm with IL-2

ch14.18/CHO

Intervention Type DRUG

ch14.18/CHO antibody is given during MRD treatment

Interventions

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Vincristine

given during Rapid COJEC and modified N7 therapy

Intervention Type DRUG

Aldesleukin

Aldesleukin is given during MRD Treatment for patients randomised to the arm with IL-2

Intervention Type DRUG

ch14.18/CHO

ch14.18/CHO antibody is given during MRD treatment

Intervention Type DRUG

Carboplatin

Carboplatin is given during induction Treatment (R3 randomisation: Rapid COJEC arm)

Intervention Type DRUG

Etoposide

Etoposide is given during Induction Treatment (both R3 randomisation arms)

Intervention Type DRUG

Cisplatin

Cisplatin is given during Induction Treatment (both R3 randomisation arms)

Intervention Type DRUG

Cyclophosphamide

Cyclophosphamid is given during Induction Treatment (both R3 randomisation arms)

Intervention Type DRUG

Doxorubicin

Doxorubicin is given during Induction Treatment (R3 arm modified N7)

Intervention Type DRUG

G-CSF

G-CSF is given during Induction Treatment

Intervention Type DRUG

Busulfan

In case i.v. busulfan is not available, the use of oral busulfan is permitted, although not recommended.

Intervention Type DRUG

Melphalan

Melphalan is given during MAT treatment

Intervention Type DRUG

Other Intervention Names

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Interleukin 2, IL-2, IL2 anti GD2 antibody Dinutuximab beta EUSA Qarziba® Paraplatin VP16 CDDP Endoxan Adriamycin Filgrastim Busilvex Myleran Busulphan Alkeran

Eligibility Criteria

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Inclusion Criteria

* • Established diagnosis of neuroblastoma according to the International Neuroblastoma Staging System (INSS).

* Age below 21 years.
* High risk neuroblastoma defined as either:

1. INSS stage 2, 3, 4, and 4s with MYCN amplification, or
2. INSS stage 4 without MYCN amplification aged \> 12 months at diagnosis
* Patients who have received no previous chemotherapy except for one cycle of etoposide and carboplatin (VP16/Carbo). In this situation patients will receive Rapid COJEC induction and the first Rapid COJEC cycle may be replaced by the first cycle VP16/Carbo (etoposide / carboplatin).
* Written informed consent, including agreement of parents or legal guardian for minors, to enter a randomised study if the criteria for randomisation are met.
* Tumour cell material available for determination of biological prognostic factors.
* Females of childbearing potential must have a negative pregnancy test. Patients of childbearing potential must agree to use an effective birth control method. Female patients who are lactating must agree to stop breast-feeding.
* Registration of all eligibility criteria with the data centre within 6 weeks from diagnosis.
* Provisional follow up of 5 years.
* National and local ethical committee approval.


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Minimum Eligible Age

1 Month

Maximum Eligible Age

21 Years

Eligible Sex

ALL

Accepts Healthy Volunteers

No

Sponsors

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St. Anna Kinderkrebsforschung

OTHER

Sponsor Role lead

Responsible Party

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Responsibility Role SPONSOR

Principal Investigators

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Ruth L Ladenstein, MD, MBA, cPM

Role: PRINCIPAL_INVESTIGATOR

St. Anna Kinderkrebsforschung

Locations

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Ospedale dei Bambini, Palermo

Palermo, , Italy

Site Status RECRUITING

Ospedale Bambino Gesu

Rome, , Italy

Site Status RECRUITING

Azienda Ospedaliera Universitaria di Parma-Oncoematologia Pediatrica

Parma, , Italy

Site Status RECRUITING

Policlinico San Matteo

Pavia, , Italy

Site Status RECRUITING

Women and Children´s Hospital

Adelaide, , Australia

Site Status RECRUITING

Lady Cilento Children´s Hospital

Brisbane, , Australia

Site Status RECRUITING

John Hunter Children's Hospital

Newcastle, , Australia

Site Status RECRUITING

Royal Children's Hospital Melbourne

Parkville, , Australia

Site Status RECRUITING

Sydney Children's Hospital

Sydney, , Australia

Site Status RECRUITING

Children´s Hospital Westmead

Westmead, , Australia

Site Status RECRUITING

St. Anna Kinderspital

Vienna, Austra, Austria

Site Status RECRUITING

Univ.-Klinik für Kinder- und Jugendheilkunde Graz

Graz, , Austria

Site Status RECRUITING

Univ.Klinik f. Kinder-u. Jugendheilkunde Innsbruck

Innsbruck, , Austria

Site Status RECRUITING

Landes- Kinderklinik Linz

Linz, , Austria

Site Status RECRUITING

St. Johanns Spital LKH Salzburg

Salzburg, , Austria

Site Status RECRUITING

Cliniques universitaires St-Luc

Brussels, , Belgium

Site Status RECRUITING

Hôpital des Enfants

Brussels, , Belgium

Site Status RECRUITING

University Hospital Gent

Ghent, , Belgium

Site Status RECRUITING

UZ Gasthuisberg

Leuven, , Belgium

Site Status RECRUITING

CHR Citadelle

Liège, , Belgium

Site Status RECRUITING

Clinique de l'Espérance

Montegnée, , Belgium

Site Status RECRUITING

University Hospital Motol

Prague, , Czechia

Site Status RECRUITING

Aarhus Universitetshospital

Aarhus, , Denmark

Site Status RECRUITING

National State Hospital

Copenhagen, , Denmark

Site Status RECRUITING

University Hospital of Odense

Odense, , Denmark

Site Status RECRUITING

Skejby Hospital

Skejby, , Denmark

Site Status RECRUITING

Hopital d'Enfants Dijon

Dijon, , France

Site Status RECRUITING

CHU de Grenoble

Grenoble, , France

Site Status RECRUITING

CHR Pellegrin

Le Pellerin, , France

Site Status RECRUITING

Centre Oscar Lambret de Lille

Lille, , France

Site Status RECRUITING

Ospedale Civile Spirito Santo

Pescara, , Italy

Site Status RECRUITING

Ospedale "Infermi "

Rimini, , Italy

Site Status RECRUITING

Hopitaux de Marseille La Timone

Marseille, , France

Site Status RECRUITING

CHR de Nantes

Nantes, , France

Site Status RECRUITING

Hôpital Trousseau Paris

Paris, , France

Site Status RECRUITING

Institut Curie

Paris, , France

Site Status RECRUITING

Hôpital American Memorial Hospital

Reims, , France

Site Status RECRUITING

CHU-Saint Etienne

Saint-Etienne, , France

Site Status RECRUITING

Hôpital de Hautepierre

Strasbourg, , France

Site Status RECRUITING

Hôpital D'Enfants de Toulouse

Toulouse, , France

Site Status RECRUITING

Institut Gustave Roussy

Villejuif, , France

Site Status RECRUITING

"A&P Kyriakou" Children's Hospital

Athens, , Greece

Site Status RECRUITING

Aghia Sophia Children's Hospital

Athens, , Greece

Site Status RECRUITING

MITERA Hospital

Heraklion, , Greece

Site Status RECRUITING

PEPAGNH University Hospital

Heraklion, , Greece

Site Status RECRUITING

Madarász Children Hospital Budapest

Budapest, , Hungary

Site Status RECRUITING

Semmelweis University of Budapest

Budapest, , Hungary

Site Status RECRUITING

University of Debrecen

Debrecen, , Hungary

Site Status RECRUITING

University of Pecs

Pécs, , Hungary

Site Status RECRUITING

University of Szeged

Szeged, , Hungary

Site Status RECRUITING

Dublin: OLHSC

Dublin, , Ireland

Site Status RECRUITING

Rambam Medical Centre

Haifa, , Israel

Site Status RECRUITING

Schneider Children's Medical Center of Israel

Petah Tikva, , Israel

Site Status RECRUITING

Sheba Medical Center

Tel Aviv, , Israel

Site Status RECRUITING

Ospedale G. Salesi

Ancona, , Italy

Site Status RECRUITING

Universitŕ degli studi di Bari

Bari, , Italy

Site Status RECRUITING

Ospedali Riuniti

Bergamo, , Italy

Site Status RECRUITING

Ospedale S. Orsola

Bologna, , Italy

Site Status RECRUITING

Ospedale Regionale per le Microcitemie

Cagliari, , Italy

Site Status RECRUITING

Azienda Ospedaliera di Cosenza

Cosenza, , Italy

Site Status RECRUITING

Azienda Ospedaliera A. Meyer

Florence, , Italy

Site Status RECRUITING

Istituto Giannina Gaslini

Genoa, , Italy

Site Status RECRUITING

Policlinico Borgo Roma

Roma, , Italy

Site Status RECRUITING

Istituto Nazionale Tumori di Milano

Milan, , Italy

Site Status RECRUITING

Azienda Ospedal. Univ. di Modena

Modena, , Italy

Site Status RECRUITING

Sec. Univ. degli Studi di Napoli - Policlinico

Napoli, , Italy

Site Status RECRUITING

Clinica di Oncoematologia Pediatrica Padova

Padua, , Italy

Site Status RECRUITING

Casa Sollievo della Sofferenza

San Giovanni Rotondo, , Italy

Site Status RECRUITING

O.I.R.M. - S. Anna

Torino, , Italy

Site Status RECRUITING

Istituto per l'Infanzia "Burlo Garofolo"

Trieste, , Italy

Site Status RECRUITING

Haukeland University Hospital

Bergen, , Norway

Site Status RECRUITING

Rikshospitalet

Oslo, , Norway

Site Status RECRUITING

University Hospital of North-Norway

Tromsø, , Norway

Site Status RECRUITING

Medical University of Bialystok

Bialystok, , Poland

Site Status RECRUITING

Medical University of Bydgoszcz

Bydgoszcz, , Poland

Site Status RECRUITING

Childrens' Hospital in Chorzów

Chorzów, , Poland

Site Status RECRUITING

Medical University in Gdansk

Gdansk, , Poland

Site Status RECRUITING

Upper Silesian Centre of Child and Mother's Care

Katowice, , Poland

Site Status RECRUITING

University Children's Hospital

Krakow, , Poland

Site Status RECRUITING

Children's University Hospital in Lublin

Lublin, , Poland

Site Status RECRUITING

University of Medical Sciences Poznan

Poznan, , Poland

Site Status RECRUITING

Institute Mother and Child

Warsaw, , Poland

Site Status RECRUITING

Wroclaw Medical University

Wroclaw, , Poland

Site Status RECRUITING

Ipofg-Crl

Lisbon, , Portugal

Site Status RECRUITING

University Hospital F. D. Roosevelt

Banská Bystrica, , Slovakia

Site Status RECRUITING

University Children's Hospital Ljubljana

Ljubljana, , Slovenia

Site Status RECRUITING

H . Materno-Infantil Teresa Herrera

A Coruña, , Spain

Site Status RECRUITING

H. General de Alicante

Alicante, , Spain

Site Status RECRUITING

Hospital Vall d'Hebron

Barcelona, , Spain

Site Status RECRUITING

Hospital de Cruces

Bilbao, , Spain

Site Status RECRUITING

Complejo Hospitalario de Jaen

Jaén, , Spain

Site Status RECRUITING

H. Monteprincipe

Madrid, , Spain

Site Status RECRUITING

Hospital 12 de Octubre

Madrid, , Spain

Site Status RECRUITING

H Central de Asturias

Oviedo, , Spain

Site Status RECRUITING

H. C. U. de Salamanca

Salamanca, , Spain

Site Status RECRUITING

H. de Donostia Ntra. Sra. de Aranzazu

San Sebastián, , Spain

Site Status RECRUITING

H. General de Galicia

Santiago de Compostela, , Spain

Site Status RECRUITING

Hospital Virgen del Rocio

Seville, , Spain

Site Status RECRUITING

Carlos Haya

Valencia, , Spain

Site Status RECRUITING

Hospital Infantil La Fe

Valencia, , Spain

Site Status RECRUITING

H Clinico-Universitario

Zaragoza, , Spain

Site Status RECRUITING

Queen Silvia's Children's Hospital

Göteburg, , Sweden

Site Status RECRUITING

Childrens Hospital Linkoping

Linköping, , Sweden

Site Status RECRUITING

University Children's Hospital

Geneva, , Switzerland

Site Status RECRUITING

CHUV

Lausanne, , Switzerland

Site Status RECRUITING

Aberdeen: Royal Aberdeen Children's Hospital

Aberdeen, , United Kingdom

Site Status RECRUITING

Royal Belfast Hospital for Sick Children

Belfast, , United Kingdom

Site Status RECRUITING

Birmingham Children's Hospital

Birmingham, , United Kingdom

Site Status RECRUITING

Bristol Royal Hospital for Children

Bristol, , United Kingdom

Site Status RECRUITING

Addenbrooke's NHS Trust

Cambridge, , United Kingdom

Site Status RECRUITING

Llandough Hospital

Cardiff, , United Kingdom

Site Status RECRUITING

Edinburgh Royal Hospital for Sick Children

Edinburgh, , United Kingdom

Site Status RECRUITING

Glasgow Royal Hospital for Sick Children

Glasgow, , United Kingdom

Site Status RECRUITING

Leeds: St James's University Hospital

Leeds, , United Kingdom

Site Status RECRUITING

Leicester Royal Infirmary

Leicester, , United Kingdom

Site Status RECRUITING

Liverpool: Alder Hey Children's Hospital

Liverpool, , United Kingdom

Site Status RECRUITING

Great Ormond Street Hospital

London, , United Kingdom

Site Status RECRUITING

St Bartholomew's Hospital

London, , United Kingdom

Site Status RECRUITING

UCLH University College London Hospital

London, , United Kingdom

Site Status RECRUITING

Royal Manchester Children's Hospital

Manchester, , United Kingdom

Site Status RECRUITING

Newcastle: Royal Victoria Infirmary

Newcastle, , United Kingdom

Site Status RECRUITING

Nottingham: Queen's Medical Centre

Nottingham, , United Kingdom

Site Status RECRUITING

Oxford: John Radcliffe Hospital

Oxford, , United Kingdom

Site Status RECRUITING

Sheffield Children's Hospital

Sheffield, , United Kingdom

Site Status RECRUITING

Southampton General Hospital

Southhampton, , United Kingdom

Site Status RECRUITING

Royal Marsden Hospital

Sutton, , United Kingdom

Site Status RECRUITING

Countries

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Australia Austria Belgium Czechia Denmark France Greece Hungary Ireland Israel Italy Norway Poland Portugal Slovakia Slovenia Spain Sweden Switzerland United Kingdom

Central Contacts

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Ruth L Ladenstein, MD, MBA, cPM

Role: CONTACT

0043140470 ext. 4750

Facility Contacts

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Ruth Ladenstein, MD, MBA, cPM

Role: primary

0043140470 ext. 4750

MD

Role: primary

MD

Role: primary

References

Explore related publications, articles, or registry entries linked to this study.

Ladenstein R, Valteau-Couanet D, Brock P, Yaniv I, Castel V, Laureys G, Malis J, Papadakis V, Lacerda A, Ruud E, Kogner P, Garami M, Balwierz W, Schroeder H, Beck-Popovic M, Schreier G, Machin D, Potschger U, Pearson A. Randomized Trial of prophylactic granulocyte colony-stimulating factor during rapid COJEC induction in pediatric patients with high-risk neuroblastoma: the European HR-NBL1/SIOPEN study. J Clin Oncol. 2010 Jul 20;28(21):3516-24. doi: 10.1200/JCO.2009.27.3524. Epub 2010 Jun 21.

Reference Type RESULT
PMID: 20567002 (View on PubMed)

Ladenstein R, Potschger U, Pearson ADJ, Brock P, Luksch R, Castel V, Yaniv I, Papadakis V, Laureys G, Malis J, Balwierz W, Ruud E, Kogner P, Schroeder H, de Lacerda AF, Beck-Popovic M, Bician P, Garami M, Trahair T, Canete A, Ambros PF, Holmes K, Gaze M, Schreier G, Garaventa A, Vassal G, Michon J, Valteau-Couanet D; SIOP Europe Neuroblastoma Group (SIOPEN). Busulfan and melphalan versus carboplatin, etoposide, and melphalan as high-dose chemotherapy for high-risk neuroblastoma (HR-NBL1/SIOPEN): an international, randomised, multi-arm, open-label, phase 3 trial. Lancet Oncol. 2017 Apr;18(4):500-514. doi: 10.1016/S1470-2045(17)30070-0. Epub 2017 Mar 2.

Reference Type RESULT
PMID: 28259608 (View on PubMed)

Ladenstein R, Potschger U, Valteau-Couanet D, Luksch R, Castel V, Yaniv I, Laureys G, Brock P, Michon JM, Owens C, Trahair T, Chan GCF, Ruud E, Schroeder H, Beck Popovic M, Schreier G, Loibner H, Ambros P, Holmes K, Castellani MR, Gaze MN, Garaventa A, Pearson ADJ, Lode HN. Interleukin 2 with anti-GD2 antibody ch14.18/CHO (dinutuximab beta) in patients with high-risk neuroblastoma (HR-NBL1/SIOPEN): a multicentre, randomised, phase 3 trial. Lancet Oncol. 2018 Dec;19(12):1617-1629. doi: 10.1016/S1470-2045(18)30578-3. Epub 2018 Nov 12.

Reference Type RESULT
PMID: 30442501 (View on PubMed)

Morgenstern DA, Potschger U, Moreno L, Papadakis V, Owens C, Ash S, Pasqualini C, Luksch R, Garaventa A, Canete A, Elliot M, Wieczorek A, Laureys G, Kogner P, Malis J, Ruud E, Beck-Popovic M, Schleiermacher G, Valteau-Couanet D, Ladenstein R. Risk stratification of high-risk metastatic neuroblastoma: A report from the HR-NBL-1/SIOPEN study. Pediatr Blood Cancer. 2018 Nov;65(11):e27363. doi: 10.1002/pbc.27363. Epub 2018 Jul 17.

Reference Type RESULT
PMID: 30015396 (View on PubMed)

Berbegall AP, Bogen D, Potschger U, Beiske K, Bown N, Combaret V, Defferrari R, Jeison M, Mazzocco K, Varesio L, Vicha A, Ash S, Castel V, Coze C, Ladenstein R, Owens C, Papadakis V, Ruud E, Amann G, Sementa AR, Navarro S, Ambros PF, Noguera R, Ambros IM. Heterogeneous MYCN amplification in neuroblastoma: a SIOP Europe Neuroblastoma Study. Br J Cancer. 2018 May;118(11):1502-1512. doi: 10.1038/s41416-018-0098-6. Epub 2018 May 14.

Reference Type RESULT
PMID: 29755120 (View on PubMed)

Mueller I, Ehlert K, Endres S, Pill L, Siebert N, Kietz S, Brock P, Garaventa A, Valteau-Couanet D, Janzek E, Hosten N, Zinke A, Barthlen W, Varol E, Loibner H, Ladenstein R, Lode HN. Tolerability, response and outcome of high-risk neuroblastoma patients treated with long-term infusion of anti-GD2 antibody ch14.18/CHO. MAbs. 2018 Jan;10(1):55-61. doi: 10.1080/19420862.2017.1402997. Epub 2017 Dec 5.

Reference Type RESULT
PMID: 29120699 (View on PubMed)

Ladenstein R, Potschger U, Valteau-Couanet D, Luksch R, Castel V, Ash S, Laureys G, Brock P, Michon JM, Owens C, Trahair T, Chi Fung Chan G, Ruud E, Schroeder H, Beck-Popovic M, Schreier G, Loibner H, Ambros P, Holmes K, Castellani MR, Gaze MN, Garaventa A, Pearson ADJ, Lode HN. Investigation of the Role of Dinutuximab Beta-Based Immunotherapy in the SIOPEN High-Risk Neuroblastoma 1 Trial (HR-NBL1). Cancers (Basel). 2020 Jan 28;12(2):309. doi: 10.3390/cancers12020309.

Reference Type RESULT
PMID: 32013055 (View on PubMed)

Bellini A, Potschger U, Bernard V, Lapouble E, Baulande S, Ambros PF, Auger N, Beiske K, Bernkopf M, Betts DR, Bhalshankar J, Bown N, de Preter K, Clement N, Combaret V, Font de Mora J, George SL, Jimenez I, Jeison M, Marques B, Martinsson T, Mazzocco K, Morini M, Muhlethaler-Mottet A, Noguera R, Pierron G, Rossing M, Taschner-Mandl S, Van Roy N, Vicha A, Chesler L, Balwierz W, Castel V, Elliott M, Kogner P, Laureys G, Luksch R, Malis J, Popovic-Beck M, Ash S, Delattre O, Valteau-Couanet D, Tweddle DA, Ladenstein R, Schleiermacher G. Frequency and Prognostic Impact of ALK Amplifications and Mutations in the European Neuroblastoma Study Group (SIOPEN) High-Risk Neuroblastoma Trial (HR-NBL1). J Clin Oncol. 2021 Oct 20;39(30):3377-3390. doi: 10.1200/JCO.21.00086. Epub 2021 Jun 11.

Reference Type DERIVED
PMID: 34115544 (View on PubMed)

Holmes K, Potschger U, Pearson ADJ, Sarnacki S, Cecchetto G, Gomez-Chacon J, Squire R, Freud E, Bysiek A, Matthyssens LE, Metzelder M, Monclair T, Stenman J, Rygl M, Rasmussen L, Joseph JM, Irtan S, Avanzini S, Godzinski J, Bjornland K, Elliott M, Luksch R, Castel V, Ash S, Balwierz W, Laureys G, Ruud E, Papadakis V, Malis J, Owens C, Schroeder H, Beck-Popovic M, Trahair T, Forjaz de Lacerda A, Ambros PF, Gaze MN, McHugh K, Valteau-Couanet D, Ladenstein RL; International Society of Paediatric Oncology Europe Neuroblastoma Group (SIOPEN). Influence of Surgical Excision on the Survival of Patients With Stage 4 High-Risk Neuroblastoma: A Report From the HR-NBL1/SIOPEN Study. J Clin Oncol. 2020 Sep 1;38(25):2902-2915. doi: 10.1200/JCO.19.03117. Epub 2020 Jul 8.

Reference Type DERIVED
PMID: 32639845 (View on PubMed)

Viprey VF, Gregory WM, Corrias MV, Tchirkov A, Swerts K, Vicha A, Dallorso S, Brock P, Luksch R, Valteau-Couanet D, Papadakis V, Laureys G, Pearson AD, Ladenstein R, Burchill SA. Neuroblastoma mRNAs predict outcome in children with stage 4 neuroblastoma: a European HR-NBL1/SIOPEN study. J Clin Oncol. 2014 Apr 1;32(10):1074-83. doi: 10.1200/JCO.2013.53.3604. Epub 2014 Mar 3.

Reference Type DERIVED
PMID: 24590653 (View on PubMed)

Other Identifiers

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HR-NBL-1.8 / SIOPEN

Identifier Type: -

Identifier Source: org_study_id

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