A Study to Determine the Effect of Triheptanoin Compared With Even-Chain MCT on MCEs in Pediatric Patients With LC-FAOD

NCT ID: NCT05933200

Last Updated: 2026-01-13

Study Results

Results pending

The study team has not published outcome measurements, participant flow, or safety data for this trial yet. Check back later for updates.

Basic Information

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Recruitment Status

ACTIVE_NOT_RECRUITING

Clinical Phase

PHASE3

Total Enrollment

69 participants

Study Classification

INTERVENTIONAL

Study Start Date

2023-02-28

Study Completion Date

2027-08-31

Brief Summary

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The main goal of this study is to evaluate the effects of triheptanoin versus Medium-chain Triglycerides (MCT) on frequency of Major Clinical Events (MCEs).

Detailed Description

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Participants will be randomly assigned 1:1 to receive triheptanoin or MCT oil. The duration of the study is estimated to be 3.5 to 4 years. The study comprises the following: Screening Period, Baseline (Month 0), Double-blind Treatment Period (including Titration and End of Study Visit), Safety Follow-up Phone Visit, and an Open Access Period.

In addition, a substudy will examine the effect of triheptanoin versus MCT on decreasing liver fat fraction to avoid or improve steatosis in subjects with LC-FAOD. Participants older than 2 years of age at selected sites will be invited to screen for the Liver Substudy.

Conditions

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Long-chain Fatty Acid Oxidation Disorders (LC-FAOD)

Study Design

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Allocation Method

RANDOMIZED

Intervention Model

PARALLEL

Primary Study Purpose

TREATMENT

Blinding Strategy

QUADRUPLE

Participants Caregivers Investigators Outcome Assessors

Study Groups

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Triheptanoin

Participants will be given prescriptions for triheptanoin in mL/day, which will be divided into approximately 4 administrations per day, with precise instructions for administration. Triheptanoin will be titrated up to the first 6 weeks of the study. After titration, the dose is to remain stable for the remainder of the Double-blind Treatment Period. Following the Double-blind Treatment Period, open-label triheptanoin will be provided at participants' current dose during an Open Access Period, if no other options to receive trihepatnoin are available locally.

Group Type EXPERIMENTAL

Triheptanoin

Intervention Type DRUG

Liquid for oral (PO) or enteral feeding tube administration

MCT

Participants will be given prescriptions for MCT in mL/day, which will be divided into approximately 4 administrations per day, with precise instructions for administration. MCT will be titrated up to the first 6 weeks of the study. After titration, the dose is to remain stable for the remainder of the Double-blind Treatment Period. Following the Double-blind Treatment Period, open-label triheptanoin will be provided at participants' current dose during an Open Access Period, if no other options to receive trihepatnoin are available locally.

Group Type ACTIVE_COMPARATOR

MCT Oil

Intervention Type DIETARY_SUPPLEMENT

Liquid for oral (PO) or enteral feeding tube administration

Interventions

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MCT Oil

Liquid for oral (PO) or enteral feeding tube administration

Intervention Type DIETARY_SUPPLEMENT

Triheptanoin

Liquid for oral (PO) or enteral feeding tube administration

Intervention Type DRUG

Other Intervention Names

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UX007 Dojolvi Medium-chain Triglyceride

Eligibility Criteria

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Inclusion Criteria

* Males and females, from 0 (including newborns) to \< 18 years of age at time of randomization
* Confirmed diagnosis of LC-FAOD
* Have a caregiver(s) willing and able to assist in all applicable study requirements
* Have a legally authorized representative willing and able to provide written informed consent after the nature of the study has been explained and prior to any research-related procedures, and the study participant to be able to provide age-appropriate written assent
* Have ANY ONE of the following significant clinical manifestations of LC-FAOD:

* At least 2 in the prior year, or 3 in the prior 2 years, of severe major episodes of metabolic decompensation (eg, hypoglycemia, rhabdomyolysis, or exacerbation of cardiomyopathy, requiring ER/urgent care unit visits or hospitalizations)
* Recurrent symptomatic hypoglycemia (clinical symptoms of hypoglycemia) requiring intervention
* Susceptibility to hypoglycemia after short periods of fasting (less than 4 to 12 hours, depending on age)
* Evidence of functional cardiomyopathy requiring ongoing medical management or clinical manifestation of heart failure
* Sibling(s) with the same pathogenic variant who presented with MCEs
* Participant with pathogenic variants that are known or suspected to be associated with absent or severely reduced enzyme activity or with severe disease manifestations.
* From the period following informed consent to 5 days after the last dose of study drug, females of childbearing potential and fertile males must consent to use highly effective contraception. If female, agree not to become pregnant. If male, agree not to father a child or donate sperm


* Enrollment in the Main Study of Study UX007-CL302
* Age \> 2 years
* Liver fat content ≥ 2% and \< 20% PDFF as assessed by 1 H-MRS
* Body mass index \< 95th percentile
* Able to comply with instructions (remaining still during scan) and requirements (eg, constraints on recent meals, no metallic items or implanted devices in the body, no recent contrast agents) for liver 1 H-MRS scan

Exclusion Criteria

* Enrolled in a clinical study involving concurrent use of an investigational drug product within 30 days before Screening
* Use of a prohibited medication (eg, valproate products or pancreatic lipase inhibitors) within 30 days before Screening, or unwilling to avoid a prohibited medication or other substance that may confound study objectives
* Treatment with triheptanoin within 60 days of Screening
* History of known hypersensitivity to triheptanoin or MCT or its excipients that, in the judgement of the Investigator, places the subject at increased risk for adverse effects
* Caregiver unwilling or unable to sign informed consent, or release of medical records, or follow study procedures
* Have any comorbid conditions, including unstable major organ-system disease(s), that in the opinion of the Investigator places the subject at increased risk of complications, interferes with study participation or compliance, or confounds study objectives or interpretation of results. History of metabolic decompensation(s) with metabolic acidosis, hyperammonemia, and/or liver enzyme elevations does not constitute an exclusion criterion unless in the opinion of the Investigator places the subject at increased risk of complications, interferes with study participation or compliance, or confounds study objectives or interpretation of results.
* Have a diagnosis of pancreatic insufficiency
* Pregnant, breastfeeding, or planning to become pregnant (self or partner) at any time during the study


* Acute or chronic liver disease other than LC-FAOD that presents with increased risk of liver fat (eg, hepatic cirrhosis, viral toxic or drug hepatitis, diabetes mellitus) and/or metabolic syndrome
* Need for anesthesia/sedation to perform liver 1 H-MRS
Maximum Eligible Age

17 Years

Eligible Sex

ALL

Accepts Healthy Volunteers

No

Sponsors

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Ultragenyx Pharmaceutical Inc

INDUSTRY

Sponsor Role lead

Responsible Party

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Responsibility Role SPONSOR

Principal Investigators

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Medical Director

Role: STUDY_DIRECTOR

Ultragenyx Pharmaceutical Inc

Locations

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General University Hospital in Prague-GUH (Všeobecná fakultní nemocnice v Praze- VFN)

Prague, , Czechia

Site Status

Universitätsklinikum Freiburg

Freiburg im Breisgau, , Germany

Site Status

Juntendo University Hospital

Bunkyo City, Tokyo, Japan

Site Status

The Jikei University Hospital

Minato, Tokyo, Japan

Site Status

Instytut Pomnik-Centrum Zdrowia Dziecka

Warsaw, Masovian Voivodeship, Poland

Site Status

Gdańksi Uniwersytet Medyczny

Gdansk, Pomeranian Voivodeship, Poland

Site Status

King Faisal Specialist Hospital & Research Centre

Riyadh, , Saudi Arabia

Site Status

Sant Joan de Deu Hospital (SJD)

Barcelona, Esplugues de Llobregat, Spain

Site Status

University Hospital Santiago de Compostela

A Coruña, , Spain

Site Status

University Hospital 12 de Octubre

Madrid, , Spain

Site Status

Cukurova University

Adana, , Turkey (Türkiye)

Site Status

Gazi University

Ankara, , Turkey (Türkiye)

Site Status

Ege University

Bornova-İzmir, , Turkey (Türkiye)

Site Status

Istanbul Universitesi Istanbul Tip Fakultesi Hastanesi

Istanbul, , Turkey (Türkiye)

Site Status

Cerrahpasa Medical Faculty

Istanbul, , Turkey (Türkiye)

Site Status

Countries

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Czechia Germany Japan Poland Saudi Arabia Spain Turkey (Türkiye)

Related Links

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Other Identifiers

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2022-001539-10

Identifier Type: EUDRACT_NUMBER

Identifier Source: secondary_id

2023-509809-76-00

Identifier Type: CTIS

Identifier Source: secondary_id

UX007-CL302

Identifier Type: -

Identifier Source: org_study_id

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