A Study of OV101 in Individuals With Angelman Syndrome (AS)

NCT ID: NCT04106557

Last Updated: 2024-01-08

Study Results

Results available

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Basic Information

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Recruitment Status

COMPLETED

Clinical Phase

PHASE3

Total Enrollment

104 participants

Study Classification

INTERVENTIONAL

Study Start Date

2019-09-09

Study Completion Date

2020-11-02

Brief Summary

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The purpose of this study is to assess the efficacy and safety of oral OV101 (gaboxadol) in pediatric subjects with Angelman syndrome.

Detailed Description

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Conditions

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Primary Disease or Condition Being Studied: Angelman Syndrome (AS)

Study Design

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Allocation Method

RANDOMIZED

Intervention Model

PARALLEL

Primary Study Purpose

TREATMENT

Blinding Strategy

DOUBLE

Participants Investigators
Double (Participant/Care Giver and Investigator/Outcomes Assessor)

Study Groups

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OV101 once daily (weight-based dosing) Other Name:Gaboxadol

OV101 (gaboxadol), oral, provided once daily at bedtime for 12 week duration

Group Type EXPERIMENTAL

Gaboxadol

Intervention Type DRUG

OV101 versus placebo once daily at bedtime for 12 weeks

Placebo once daily

Matching placebo,oral, provided once daily at bedtime for 12 week duration

Group Type PLACEBO_COMPARATOR

Placebo

Intervention Type DRUG

Matching placebo capsules to OV101 capsules.

Interventions

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Gaboxadol

OV101 versus placebo once daily at bedtime for 12 weeks

Intervention Type DRUG

Placebo

Matching placebo capsules to OV101 capsules.

Intervention Type DRUG

Eligibility Criteria

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Inclusion Criteria

* Male or female and 2 to 12 years old (inclusive) at the time of informed consent
* Confirmed molecular diagnosis of AS
* Has a CGI-S-AS score of 3 or more at baseline.
* Meets the following age-appropriate body weight criterion:

1. Subjects 2 to 3 years old must have a minimum body weight of 9 kg.
2. Subjects 4 years and older must be between 17 kg and 64 kg (inclusive).
* Stable concomitant mediations for at least 4 weeks before study start

Exclusion Criteria

* Any condition that would limit study participation
* Clinically significant lab or vital sign abnormalities at the time of screening
* Poorly controlled seizures (weekly seizures of any frequency with a duration more than 3 minutes, weekly seizures occurring more than 3 times per week, each with a duration of less than 3 minutes, or as defined by investigator assessment)
* Use of prescription medications for sleep, minocycline, or levodopa within the 4 weeks prior to Day 1 or during the study. Benzodiazepines chronically administered for seizure control are permitted.
* Cannot comply with protocol study assessments during screening or caregiver unable to comply with study requirements.
* Enrolled in any clinical trial or used any investigational agent within the 30 days before screening or concurrently with this study.
Minimum Eligible Age

2 Years

Maximum Eligible Age

12 Years

Eligible Sex

ALL

Accepts Healthy Volunteers

No

Sponsors

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Healx AI

INDUSTRY

Sponsor Role lead

Responsible Party

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Responsibility Role SPONSOR

Locations

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Ovid Therapeutics Investigative Site

Phoenix, Arizona, United States

Site Status

Ovid Therapeutics Investigative Site

San Diego, California, United States

Site Status

Ovid Therapeutics Investigative Site

Chicago, Illinois, United States

Site Status

Ovid Therapeutics Investigative Site

Boston, Massachusetts, United States

Site Status

Ovid Therapeutics Investigative Site

Lexington, Massachusetts, United States

Site Status

Ovid Therapeutics Investigative Site

Cincinnati, Ohio, United States

Site Status

Ovid Therapeutics Investigative Site

Media, Pennsylvania, United States

Site Status

Ovid Therapeutics Investigative Site

Nashville, Tennessee, United States

Site Status

Ovid Therapeutics Investigative Site

Tacoma, Washington, United States

Site Status

Ovid Therapeutics Investigative Site

Brisbane, Queensland, Australia

Site Status

Ovid Therapeutics Investigative Site

Heidelberg, Victoria, Australia

Site Status

Ovid Therapeutics Investigative Site

Munich, , Germany

Site Status

Ovid Therapeutics Investigative Site

Ramat Gan, , Israel

Site Status

Ovid Therapeutics Investigative Site

Rotterdam, , Netherlands

Site Status

Countries

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United States Australia Germany Israel Netherlands

References

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Keary C, Bird LM, de Wit MC, Hatti S, Heimer G, Heussler H, Kolevzon A, Mathews A, Ochoa-Lubinoff C, Tan WH, Yan Y, Adams M. Gaboxadol in angelman syndrome: A double-blind, parallel-group, randomized placebo-controlled phase 3 study. Eur J Paediatr Neurol. 2023 Nov;47:6-12. doi: 10.1016/j.ejpn.2023.07.008. Epub 2023 Aug 1.

Reference Type DERIVED
PMID: 37639777 (View on PubMed)

Provided Documents

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Document Type: Study Protocol

View Document

Document Type: Statistical Analysis Plan

View Document

Other Identifiers

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OV101-19-001

Identifier Type: -

Identifier Source: org_study_id

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