An Open-label Extension Study of an Investigational Drug, Fitusiran, in Patients With Moderate or Severe Hemophilia A or B

NCT ID: NCT02554773

Last Updated: 2024-06-05

Study Results

Results available

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Basic Information

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Recruitment Status

COMPLETED

Clinical Phase

PHASE1/PHASE2

Total Enrollment

34 participants

Study Classification

INTERVENTIONAL

Study Start Date

2015-09-18

Study Completion Date

2023-03-21

Brief Summary

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Primary Objective:

To evaluate the long-term safety and tolerability of fitusiran in male patients with moderate or severe hemophilia A or B

Secondary Objectives:

* To investigate the long-term efficacy of fitusiran
* To characterize the safety and efficacy of concomitantly administered Factor VIII (FVIII), Factor IX (FIX) or bypassing agents (BPA) and fitusiran for treatment of bleeding episodes
* To assess changes in health-related quality of life (QOL) over time
* To characterize antithrombin (AT) reduction and thrombin generation (TG) increase
* To characterize the pharmacokinetics (PK) of fitusiran

Detailed Description

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It is anticipated that patients in this study will receive treatment with open label fitusiran for approximately 7 years or until fitusiran becomes commercially available, whichever occurs first.

Conditions

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Hemophilia A Hemophilia B

Study Design

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Allocation Method

NA

Intervention Model

SINGLE_GROUP

Primary Study Purpose

TREATMENT

Blinding Strategy

NONE

Study Groups

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Fitusiran

Patients will be administered subcutaneous (SC) fitusiran once monthly or every 2 months according to the dose selection rules defined in protocol.

Group Type EXPERIMENTAL

Fitusiran (SAR439774)

Intervention Type DRUG

Pharmaceutical form: solution for injection Route of administration : subcutaneous (sc)

Interventions

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Fitusiran (SAR439774)

Pharmaceutical form: solution for injection Route of administration : subcutaneous (sc)

Intervention Type DRUG

Eligibility Criteria

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Inclusion Criteria

* Completed and tolerated study drug dosing in study TDR14767 (ALN-AT3SC-001)
* Male aged ≥18 years
* Moderate or severe, clinically stable hemophilia A or B as evidenced by a laboratory FVIII or FIX level ≤5% at screening. Patients with a FVIII or FIX level \>5% at screening will be eligible on provision of a historic laboratory report indicating a trough level ≤5%
* Willing and able to comply with the study requirements and provide written informed consent

Exclusion Criteria

* Clinically significant liver disease
* Patients known to be human immunodeficiency virus seropositive and have a CD4 count \<200 cells/μL
* History of venous thromboembolism
* Current serious mental illness that, in the judgment of the Investigator, may compromise patient safety, ability to participate in all study assessments, or study integrity
* Clinically relevant history or presence of cardiovascular, respiratory, gastrointestinal, renal, neurological, inflammatory, or other diseases that, in the judgment of the Investigator, precludes study participation
Minimum Eligible Age

18 Years

Eligible Sex

MALE

Accepts Healthy Volunteers

No

Sponsors

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Genzyme, a Sanofi Company

INDUSTRY

Sponsor Role lead

Responsible Party

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Responsibility Role SPONSOR

Principal Investigators

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Clinical Sciences & Operations, MD

Role: STUDY_DIRECTOR

Sanofi

Locations

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Clinical Trial Site

Ann Arbor, Michigan, United States

Site Status

Clinical Trial Site

Pittsburgh, Pennsylvania, United States

Site Status

Clinical Trial Site

Plovdiv, , Bulgaria

Site Status

Clinical Trial Site

Sofia, , Bulgaria

Site Status

Clinical Trial Site

Kirov, , Russia

Site Status

Clinical Trial Site

Moscow, , Russia

Site Status

Clinical Trial Site

Zurich, , Switzerland

Site Status

Clinical Trial Site

Basingstoke, , United Kingdom

Site Status

Clinical Trial Site

Glasgow, , United Kingdom

Site Status

Clinical Trial Site

London, , United Kingdom

Site Status

Clinical Trial Site

London, , United Kingdom

Site Status

Clinical Trial Site

Truro, , United Kingdom

Site Status

Countries

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United States Bulgaria Russia Switzerland United Kingdom

References

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Pipe SW, Lissitchkov T, Georgiev P, Mangles S, Hegemann I, Trinchero A, Chowdary P, Forbes A, Feng L, Menapace LA, Kichou S, Andersson S, Demissie M, Ragni MV. Long-term safety and efficacy of fitusiran prophylaxis, and perioperative management, in people with hemophilia A or B. Blood Adv. 2025 Mar 11;9(5):1147-1158. doi: 10.1182/bloodadvances.2024013900.

Reference Type DERIVED
PMID: 39642315 (View on PubMed)

Provided Documents

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Document Type: Study Protocol

View Document

Document Type: Statistical Analysis Plan

View Document

Other Identifiers

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ALN-AT3SC-002

Identifier Type: OTHER

Identifier Source: secondary_id

2015-001395-21

Identifier Type: EUDRACT_NUMBER

Identifier Source: secondary_id

U1111-1251-5204

Identifier Type: REGISTRY

Identifier Source: secondary_id

LTE14762

Identifier Type: -

Identifier Source: org_study_id

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