Prenatal Microarray Follow-Up Study

NCT ID: NCT02160938

Last Updated: 2019-03-25

Study Results

Results pending

The study team has not published outcome measurements, participant flow, or safety data for this trial yet. Check back later for updates.

Basic Information

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Recruitment Status

COMPLETED

Total Enrollment

184 participants

Study Classification

OBSERVATIONAL

Study Start Date

2013-02-28

Study Completion Date

2018-12-31

Brief Summary

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The objectives of this multi-center collaborative study are to ascertain the frequency of specific copy number variants (CNVs) identified prenatally and to evaluate in detail through continued follow-up of the children the phenotypes associated with CNVs of known or uncertain clinical significance.

Detailed Description

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Specifically the aims are as follows:

1. Determine the intellectual function of the children at age 3 years
2. Determine phenotypic characteristics other than intellectual function of the children at age 3 years
3. Determine the frequency of specific copy number variants discovered during routine prenatal diagnostic testing
4. Evaluate the educational, counseling and psychosocial implications of microarray testing as it is introduced as a standard prenatal diagnostic procedure.

Conditions

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Genetic Diseases

Study Design

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Observational Model Type

COHORT

Study Time Perspective

PROSPECTIVE

Study Groups

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3 year follow-up cohort

When the infants reach 24 months of age, the Study Follow-up Specialist will send all participants an age- appropriate Ages and Stages Questionnaire (ASQ) for completion.

At as close to the age of 3 as possible, the following exams will be performed and are described below:

* The Vineland-II Adaptive Behavior Scale (VABS)
* Wechsler Preschool and Primary Scale of Intelligence IV (WPPSI-IV), or Wechsler Intelligence Scale for Children - Fifth Edition (WISC-V, for siblings older than 7 years 7 months, when necessary)
* Children will also be photographed (for review by the study dysmorphologist)

3-year follow-up

Intervention Type OTHER

When the infants reach 24 months of age, the Study Follow-up Specialist will send all participants an age- appropriate Ages and Stages Questionnaire (ASQ) for completion.

At the age of 3, the following exams will be performed and are described below:

* The Vineland-II Adaptive Behavior Scale (VABS)
* Wechsler Preschool and Primary Scale of Intelligence IV (WPPSI-IV), or Wechsler Intelligence Scale for Children - Fifth Edition (WISC-V, for siblings older than 7 years 7 months, when necessary)
* Children will also be photographed (for review by the study dysmorphologist)

Limited follow-up cohort

Women with children who will not reach the age of 2 years 6 months by the end of our study but have a prenatally diagnosed CNV will be recruited into the limited follow-up study. Each center will describe the study to eligible women and will verbally obtain their permission to be contacted by the Study Follow-up Specialist. The Study Follow-Up Specialist will contact the patient, explain the study, and obtain full written informed consent.

No interventions assigned to this group

Interventions

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3-year follow-up

When the infants reach 24 months of age, the Study Follow-up Specialist will send all participants an age- appropriate Ages and Stages Questionnaire (ASQ) for completion.

At the age of 3, the following exams will be performed and are described below:

* The Vineland-II Adaptive Behavior Scale (VABS)
* Wechsler Preschool and Primary Scale of Intelligence IV (WPPSI-IV), or Wechsler Intelligence Scale for Children - Fifth Edition (WISC-V, for siblings older than 7 years 7 months, when necessary)
* Children will also be photographed (for review by the study dysmorphologist)

Intervention Type OTHER

Eligibility Criteria

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Inclusion Criteria

1. Singleton or multi-fetal pregnancy with a prenatal invasive procedure resulting in a diagnosis by microarray analysis of a microdeletion/duplication less than 10 Mbs, either pathogenic or of uncertain significance, which is reported to the patient. This includes:

* Infants diagnosed during prenatal diagnostic studies performed at the10 pre-specified prenatal diagnostic centers
* Infants diagnosed by analysis of microarrays performed at the collaborating laboratories
* Infants referred through the Prenatal Microarray Resource Center website
* Children who will be at least 3 years of age by January of 2018, and who had a prenatally detected CNV \<10 Mbs, either pathogenic or of uncertain significance OR

* CNVs of uncertain or known significance, some of which were not reported to the patient
* Mosaic findings by karyotype and/or microarray alone.

Exclusion Criteria

1. Patient refusal to allow infant follow-up through the age of three
2. Patient not fluent in the English language
3. Patient under the age of 18
4. In surrogate pregnancies, the "rearing parents" are unavailable to give consent.
Minimum Eligible Age

18 Years

Eligible Sex

ALL

Accepts Healthy Volunteers

No

Sponsors

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Eunice Kennedy Shriver National Institute of Child Health and Human Development (NICHD)

NIH

Sponsor Role collaborator

National Human Genome Research Institute (NHGRI)

NIH

Sponsor Role collaborator

Columbia University

OTHER

Sponsor Role lead

Responsible Party

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Ronald J Wapner, MD

Professor and Vice Chairman for Research, Department of Obstetrics and Gynecology

Responsibility Role PRINCIPAL_INVESTIGATOR

Principal Investigators

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Ronald Wapner, MD

Role: PRINCIPAL_INVESTIGATOR

Columbia University

Locations

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Center for Fetal Medicine

Los Angeles, California, United States

Site Status

George Washington University Biostatistics Center

Rockville, Maryland, United States

Site Status

Montefiore Medical Center

Larchmont, New York, United States

Site Status

North Shore LIJ

Manhasset, New York, United States

Site Status

Mt. Sinai Medical Center

New York, New York, United States

Site Status

Columbia University

New York, New York, United States

Site Status

OB/GYN Services PC

New York, New York, United States

Site Status

Geisinger Health System

Danville, Pennsylvania, United States

Site Status

University of Pennsylvania

Philadelphia, Pennsylvania, United States

Site Status

Countries

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United States

References

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Wapner RJ, Martin CL, Levy B, Ballif BC, Eng CM, Zachary JM, Savage M, Platt LD, Saltzman D, Grobman WA, Klugman S, Scholl T, Simpson JL, McCall K, Aggarwal VS, Bunke B, Nahum O, Patel A, Lamb AN, Thom EA, Beaudet AL, Ledbetter DH, Shaffer LG, Jackson L. Chromosomal microarray versus karyotyping for prenatal diagnosis. N Engl J Med. 2012 Dec 6;367(23):2175-84. doi: 10.1056/NEJMoa1203382.

Reference Type BACKGROUND
PMID: 23215555 (View on PubMed)

Bernhardt BA, Soucier D, Hanson K, Savage MS, Jackson L, Wapner RJ. Women's experiences receiving abnormal prenatal chromosomal microarray testing results. Genet Med. 2013 Feb;15(2):139-45. doi: 10.1038/gim.2012.113. Epub 2012 Sep 6.

Reference Type BACKGROUND
PMID: 22955112 (View on PubMed)

Bernhardt BA, Kellom K, Barbarese A, Faucett WA, Wapner RJ. An exploration of genetic counselors' needs and experiences with prenatal chromosomal microarray testing. J Genet Couns. 2014 Dec;23(6):938-47. doi: 10.1007/s10897-014-9702-y. Epub 2014 Feb 27.

Reference Type RESULT
PMID: 24569858 (View on PubMed)

Other Identifiers

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5U01HD055651

Identifier Type: NIH

Identifier Source: secondary_id

View Link

AAAL0100

Identifier Type: -

Identifier Source: org_study_id

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