A Study Evaluating the Efficacy and Safety of Mitapivat (AG-348) in Participants With Sickle Cell Disease (RISE UP)

NCT ID: NCT05031780

Last Updated: 2025-12-26

Study Results

Results pending

The study team has not published outcome measurements, participant flow, or safety data for this trial yet. Check back later for updates.

Basic Information

Get a concise snapshot of the trial, including recruitment status, study phase, enrollment targets, and key timeline milestones.

Recruitment Status

ACTIVE_NOT_RECRUITING

Clinical Phase

PHASE2/PHASE3

Total Enrollment

286 participants

Study Classification

INTERVENTIONAL

Study Start Date

2022-02-11

Study Completion Date

2030-02-28

Brief Summary

Review the sponsor-provided synopsis that highlights what the study is about and why it is being conducted.

This clinical trial is a Phase 2/3 study that will determine the recommended dose of mitapivat and evaluate the efficacy and safety of mitapivat in sickle cell disease by testing how well mitapivat works compared to placebo to increase the amount of hemoglobin in the blood and to reduce or prevent the occurrence of sickle cell pain crises. In addition, the long-term effect of mitapivat on efficacy and safety will be explored in an open-label extension portion.

Detailed Description

Dive into the extended narrative that explains the scientific background, objectives, and procedures in greater depth.

Mitapivat is a small molecule, oral activator of pyruvate kinase R (PKR). PKR is involved with maintaining health, energy, and longevity of red blood cells (RBCs). The study aims to evaluate the efficacy and safety of treatment with mitapivat in participants with sickle cell disease. The study is a Phase 2/3 study in which the recommended dose of mitapivat will be selected and further evaluated. The Phase 2 portion includes a 12-week randomized, placebo-controlled period in which participants will be randomized in a 1:1:1 ratio to receive 2 dose levels of mitapivat or placebo. The Phase 3 portion includes a 52-week randomized, placebo-controlled period in which participants will be randomized in a 2:1 ratio to receive the recommended mitapivat dose level or placebo. Participants who complete either the Phase 2 or Phase 3 portion will have the option to move into a 216-week open label extension period to receive mitapivat.

Conditions

See the medical conditions and disease areas that this research is targeting or investigating.

Sickle Cell Disease

Study Design

Understand how the trial is structured, including allocation methods, masking strategies, primary purpose, and other design elements.

Allocation Method

RANDOMIZED

Intervention Model

SEQUENTIAL

Primary Study Purpose

TREATMENT

Blinding Strategy

QUADRUPLE

Participants Caregivers Investigators Outcome Assessors

Study Groups

Review each arm or cohort in the study, along with the interventions and objectives associated with them.

Phase 2: Mitapivat 50 mg BID

Double-blind Period: Mitapivat 50 milligrams (mg) twice daily (BID) for 12 weeks.

Group Type EXPERIMENTAL

Mitapivat

Intervention Type DRUG

Mitapivat tablets

Phase 2: Mitapivat 100 mg BID

Double-blind Period: Mitapivat 100 mg BID for 12 weeks.

Group Type EXPERIMENTAL

Mitapivat

Intervention Type DRUG

Mitapivat tablets

Phase 2: Placebo

Double-blind Period: Mitapivat-matching placebo for 12 weeks.

Group Type PLACEBO_COMPARATOR

Mitapivat-matching placebo

Intervention Type OTHER

Placebo to match 50 mg or 100 mg tablets

Phase 2: Open-Label Extension Period

Participants who received mitapivat 50mg BID in the double-blind period may choose to receive mitapivat 50mg BID for 216 weeks after.

Participants who received mitapivat 100mg BID in the double-blind period may choose to receive mitapivat 100 mg BID for 216 weeks after.

Participants who received mitapivat-matching placebo in the double-blind period, may be randomized to receive either mitapivat 50 mg or 100 mg BID for 216 weeks after.

Group Type EXPERIMENTAL

Mitapivat

Intervention Type DRUG

Mitapivat tablets

Phase 3: Mitapivat 100 mg BID

Double-blind Period: Mitapivat 100 mg BID for 52 weeks.

Group Type EXPERIMENTAL

Mitapivat

Intervention Type DRUG

Mitapivat tablets

Phase 3: Placebo

Double-blind Period: Mitapivat-matching placebo for 52 weeks.

Group Type PLACEBO_COMPARATOR

Mitapivat-matching placebo

Intervention Type OTHER

Placebo to match 100 mg tablets

Phase 3: Open-Label Extension Period

Participants may choose to receive mitapivat 100 mg BID for 216 weeks after the Double-blind Period.

Participants who received mitapivat-matching placebo in the double-blind period, may choose to receive mitapivat 100 mg BID for 216 weeks after the Double-blind Period.

Group Type EXPERIMENTAL

Mitapivat

Intervention Type DRUG

Mitapivat tablets

Interventions

Learn about the drugs, procedures, or behavioral strategies being tested and how they are applied within this trial.

Mitapivat

Mitapivat tablets

Intervention Type DRUG

Mitapivat-matching placebo

Placebo to match 50 mg or 100 mg tablets

Intervention Type OTHER

Mitapivat-matching placebo

Placebo to match 100 mg tablets

Intervention Type OTHER

Other Intervention Names

Discover alternative or legacy names that may be used to describe the listed interventions across different sources.

AG-348 Mitapivat Sulfate

Eligibility Criteria

Check the participation requirements, including inclusion and exclusion rules, age limits, and whether healthy volunteers are accepted.

Inclusion Criteria

* Age 16 years or older (18 years or older \[France and Germany\]); participants age 16 or 17 years must physically have completed puberty;
* Documented diagnosis of sickle cell disease (SCD) (HbSS, HbSC \[combined heterozygosity for hemoglobins S and C\], HbS/beta 0- thalassemia, HbS/ beta plus thalassemia, or other sickle cell syndrome variants);
* At least 2 SCPCs and no more than 10 SCPCs in the past 12 months;
* Hemoglobin at least 5.5 and 10.5 gram per deciliter (g/dL) at the most. Hemoglobin concentration must be based on an average of at least 2 Hb concentration measurements (separated by ≥7 days) collected during the Screening Period;
* If taking hydroxyurea, the hydroxyurea dose must be stable for at least 90 days before starting study drug. Discontinuation of hydroxyurea requires a 90-day washout prior to informed assent/consent;
* Women capable of becoming pregnant must agree to use 2 forms of contraception.

Exclusion Criteria

* Pregnant, breastfeeding, or parturient;
* Receiving regularly scheduled transfusions;
* Hepatobiliary disorders including but not limited to significant liver disease or gallbladder disease;
* Severe kidney disease;
* Prior exposure to gene therapy or prior bone marrow or stem cell transplantation;
* Currently receiving treatment with a disease-modifying therapy for SCD (eg, voxelotor, crizanlizumab, L-glutamine), with the exception of hydroxyurea. The last dose of voxelotor, crizanlizumab, and L-glutamine must have been administered at least 90 days before randomization;
* Currently receiving treatment with hematopoietic stimulating agents; the last dose must have been administered at least 90 days before starting study drug;
* Received treatment on another investigational trial within 90 days prior to start of study drug or plans to participate in another investigational drug trial;
* Taking medications that are strong inhibitors of CYP3A4/5 or strong inducers of CYP3A4 that cannot be stopped in an acceptable timeframe before starting study drug (timeframe will be discussed with your doctor).
Minimum Eligible Age

16 Years

Eligible Sex

ALL

Accepts Healthy Volunteers

No

Sponsors

Meet the organizations funding or collaborating on the study and learn about their roles.

Agios Pharmaceuticals, Inc.

INDUSTRY

Sponsor Role lead

Responsible Party

Identify the individual or organization who holds primary responsibility for the study information submitted to regulators.

Responsibility Role SPONSOR

Locations

Explore where the study is taking place and check the recruitment status at each participating site.

University of California San Diego

La Jolla, California, United States

Site Status

UCLA Health

Los Angeles, California, United States

Site Status

Children's Hospital Oakland

Oakland, California, United States

Site Status

University of Connecticut Health Center

Farmington, Connecticut, United States

Site Status

Children's National Hospital

Washington D.C., District of Columbia, United States

Site Status

MedStar Washington Hospital Center

Washington D.C., District of Columbia, United States

Site Status

Sylvester Comprehensive Cancer Center-Miami

Miami, Florida, United States

Site Status

University of Chicago Medical Center

Chicago, Illinois, United States

Site Status

Riley Hospital For Children

Indianapolis, Indiana, United States

Site Status

LSU Health Sciences Center - Shreveport

Shreveport, Louisiana, United States

Site Status

National Heart Lung and Blood Institute

Bethesda, Maryland, United States

Site Status

Kaiser Permanente - Largo Medical Center

Largo, Maryland, United States

Site Status

Massachusetts General Hospital

Boston, Massachusetts, United States

Site Status

Boston Children's Hospital

Boston, Massachusetts, United States

Site Status

Boston Medical Center & Boston University School of Medicine

Boston, Massachusetts, United States

Site Status

University of Michigan

Ann Arbor, Michigan, United States

Site Status

Children's Hospital of Michigan

Detroit, Michigan, United States

Site Status

Southern Specialty Clinic

Flowood, Mississippi, United States

Site Status

Mississippi Center for Advanced Medicine

Madison, Mississippi, United States

Site Status

Cure 4 The Kids Foundation, A Division of Roseman University of Health Sciences

Las Vegas, Nevada, United States

Site Status

East Carolina University - Brody School of Medicine

Greenville, North Carolina, United States

Site Status

Penn Medicine - University of Pennsylvania Health System

Philadelphia, Pennsylvania, United States

Site Status

St. Christopher's Hospital for Children

Philadelphia, Pennsylvania, United States

Site Status

Lifespan at Rhode Island Hospital

Providence, Rhode Island, United States

Site Status

University of Texas Health Science Center of Houston

Houston, Texas, United States

Site Status

Texas Children's Hospital

Houston, Texas, United States

Site Status

Virginia Commonwealth University

Richmond, Virginia, United States

Site Status

Seattle Cancer Care Alliance, University of Washington

Seattle, Washington, United States

Site Status

Hôpital Erasme

Anderlecht, Brussels Capital, Belgium

Site Status

Universitair Ziekenhuis Antwerpen

Edegem, Brussels Capital, Belgium

Site Status

ZAS Cadix

Antwerp, , Belgium

Site Status

CHR de la Citadelle

Liège, , Belgium

Site Status

Clinique CHC MontLégia

Liège, , Belgium

Site Status

Multihemo Servicos Medicos S/A

Recife, Pernambuco, Brazil

Site Status

Hospital de Clinicas de Porto Alegre (HCPA) - PPDS

Porto Alegre, Rio Grande do Sul, Brazil

Site Status

Hospital Sao Lucas Da Pontificia Universidade Catolica Do Rio Grande Do Sul (PUCRS)

Porto Alegre, Rio Grande do Sul, Brazil

Site Status

Hospital de Clínicas da Unicamp

Campinas, São Paulo, Brazil

Site Status

Hospital Das Clínicas da Faculdade de Medicina de Ribeirão Preto - USP

Ribeirão Preto, São Paulo, Brazil

Site Status

Praxis Pesquisa Medica

Santo André, São Paulo, Brazil

Site Status

HEMORIO Instituto Nacional de Hematologia

Rio de Janeiro, , Brazil

Site Status

Hospital das Clínicas da Faculdade de Medicina da Universidad de São Paulo

São Paulo, , Brazil

Site Status

McMaster University - St. Joseph's Healthcare Hamilton

Hamilton, Ontario, Canada

Site Status

University Health Network

Toronto, Ontario, Canada

Site Status

CHU Montreal

Montreal, Quebec, Canada

Site Status

McGill University Health Center

Montreal, Quebec, Canada

Site Status

Hopitaux de La Timone

Marseille, Bouches-du-Rhône, France

Site Status

Hôpital Pellegrin, CHU de Bordeaux

Bordeaux, Gironde, France

Site Status

CHU Guadeloupe

Pointe à Pitre, Guadeloupe, France

Site Status

Institut Universitaire du Cancer de Toulouse - Oncopole

Toulouse, Haute-Garonne, France

Site Status

CHU Hôpital Henri Mondor

Créteil, Val-de-Marne, France

Site Status

Hôpital Européen Georges Pompidou

Paris, Île-de-France Region, France

Site Status

Universitätsklinikum Essen

Essen, , Germany

Site Status

Universitätsklinikum Regensburg

Regensburg, , Germany

Site Status

HaEmek Medical Center

Afula, , Israel

Site Status

Rambam Medical Center

Haifa, Ḥeifā, Israel

Site Status

Ziv Medical Center

Safed, Ḥeifā, Israel

Site Status

A.O.R.N. "A. Cardarelli"

Napoli, Campania, Italy

Site Status

AOU dell'Università degli Studi della Campania Luigi Vanvitelli

Napoli, Campania, Italy

Site Status

Azienda Ospedaliero Universitaria Di Modena Policlinico

Modena, Emilia-Romagna, Italy

Site Status

IRCCS Ospedale Pediatrico Bambino Gesù - INCIPIT - PIN

Rome, Lazio, Italy

Site Status

Ente Ospedaliero Ospedali Galliera

Genoa, Liguria, Italy

Site Status

Azienda Ospedaliera Ospedali Riuniti Villa Sofia-Cervello

Palermo, Sicily, Italy

Site Status

Kemri Usamru

Kisumu, Western, Kenya

Site Status

Kondele Children's Hospital

Kisumu, , Kenya

Site Status

Victoria Biomedical Research Institute (VIBRI)

Kisumu, , Kenya

Site Status

KEMRI CRDR Clinical Research Clinic Nairobi

Nairobi, , Kenya

Site Status

KEMRI/CRDR Siaya Clinical Research Annex

Nairobi, , Kenya

Site Status

Strathmore University

Nairobi, , Kenya

Site Status

Gertrude's Children's Hospital

Nairobi, , Kenya

Site Status

American University of Beirut Medical Center

Beirut, Beyrouth, Lebanon

Site Status

Nini Hospital

Tarablus, Mohafazat Liban-Nord, Lebanon

Site Status

American University of Beirut Medical Center

Beirut, , Lebanon

Site Status

Hammoud Hospital University Medical Center

Sidon, , Lebanon

Site Status

Erasmus MC

Rotterdam, South Holland, Netherlands

Site Status

Universitair Medisch Centrum Utrecht

Utrecht, , Netherlands

Site Status

National Hospital Abuja

Abuja, Federal Capital Territory, Nigeria

Site Status

University of Abuja Teaching Hospital

Abuja, Federal Capital Territory, Nigeria

Site Status

Lagos University Teaching Hospital

Surulere, Lagos, Nigeria

Site Status

Sultan Qaboos University Hospital, Hematology Department, COM&HS

Muscat, Musqal, Oman

Site Status

King Khalid University Hospital

Riyadh, Ar Riya, Saudi Arabia

Site Status

King Abdullah International Medical Research Center

Riyadh, , Saudi Arabia

Site Status

Hacettepe University

Ankara, Adana, Turkey (Türkiye)

Site Status

Acibadem Adana Hospital

Seyhan, Adana, Turkey (Türkiye)

Site Status

Evelina Children's Hospital

London, City of London, United Kingdom

Site Status

Cambridge University Hospitals NHS Foundation Trust

Cambridge, , United Kingdom

Site Status

Guy's and St Thomas' NHS Foundation Trust

London, , United Kingdom

Site Status

King's College Hospital NHS Foundation Trust

London, , United Kingdom

Site Status

Hammersmith Hospital

London, , United Kingdom

Site Status

University College London Hospitals (UCLH)

London, , United Kingdom

Site Status

Manchester Royal Infirmary, Manchester University NHS Foundation Trust

Manchester, , United Kingdom

Site Status

Countries

Review the countries where the study has at least one active or historical site.

Ghana United States Belgium Brazil Canada France Germany Israel Italy Kenya Lebanon Netherlands Nigeria Oman Saudi Arabia Turkey (Türkiye) United Kingdom

References

Explore related publications, articles, or registry entries linked to this study.

Idowu M, Otieno L, Dumitriu B, Lobo CLC, Thein SL, Andemariam B, Nnodu OE, Inati A, Glaros AK, Bartolucci P, Colombatti R, Taher AT, Abboud MR, Darbari D, Ataga KI, Antmen AB, Kuo KHM, de Souza Medina S, Oluyadi A, Iyer V, Morris S, Yates AM, Shao H, Patil S, Urbstonaitis R, Zaidi AU, Gheuens S, Smith WR. Safety and efficacy of mitapivat in sickle cell disease (RISE UP): results from the phase 2 portion of a global, double-blind, randomised, placebo-controlled trial. Lancet Haematol. 2025 Jan;12(1):e35-e44. doi: 10.1016/S2352-3026(24)00319-3. Epub 2024 Dec 4.

Reference Type DERIVED
PMID: 39644907 (View on PubMed)

van Dijk MJ, Rab MAE, van Oirschot BA, Bos J, Derichs C, Rijneveld AW, Cnossen MH, Nur E, Biemond BJ, Bartels M, Jans JJM, van Solinge WW, Schutgens REG, van Wijk R, van Beers EJ. One-year safety and efficacy of mitapivat in sickle cell disease: follow-up results of a phase 2, open-label study. Blood Adv. 2023 Dec 26;7(24):7539-7550. doi: 10.1182/bloodadvances.2023011477.

Reference Type DERIVED
PMID: 37934880 (View on PubMed)

Obadina M, Wilson S, Derebail VK, Little J. Emerging Therapies and Advances in Sickle Cell Disease with a Focus on Renal Manifestations. Kidney360. 2023 Jul 1;4(7):997-1005. doi: 10.34067/KID.0000000000000162. Epub 2023 May 31.

Reference Type DERIVED
PMID: 37254256 (View on PubMed)

Other Identifiers

Review additional registry numbers or institutional identifiers associated with this trial.

2021-001674-34

Identifier Type: EUDRACT_NUMBER

Identifier Source: secondary_id

AG348-C-020

Identifier Type: -

Identifier Source: org_study_id