Trial Outcomes & Findings for Evaluation of a Recombinant Factor IX Product, APVO101, in Previously-Treated Pediatric Patients With Hemophilia B (NCT NCT03855280)

NCT ID: NCT03855280

Last Updated: 2024-05-16

Results Overview

The primary efficacy variable was the ABR while on prophylaxis to prevent bleeding episodes. The ABR was defined as the number of bleeding episodes per year.

Recruitment status

COMPLETED

Study phase

PHASE3

Target enrollment

21 participants

Primary outcome timeframe

Exposure Day 1 up to 50 exposure days (approximately 6 months)

Results posted on

2024-05-16

Participant Flow

Pediatric patients (less than 11.5 years of age at first dose) with severe to moderately severe hemophilia B. Participants had a minimum of 50 exposure days of factor IX (FIX) replacement therapy prior to enrollment.

Participant milestones

Participant milestones
Measure
APVO101 Prophylaxis - Safety Population
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
PK Phase
STARTED
21
PK Phase
PK Phase
21
PK Phase
COMPLETED
21
PK Phase
NOT COMPLETED
0
Treatment Phase
STARTED
21
Treatment Phase
COMPLETED
19
Treatment Phase
NOT COMPLETED
2
Continuation Phase
STARTED
19
Continuation Phase
COMPLETED
16
Continuation Phase
NOT COMPLETED
3

Reasons for withdrawal

Reasons for withdrawal
Measure
APVO101 Prophylaxis - Safety Population
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Treatment Phase
Adverse Event
1
Treatment Phase
Withdrawal by Subject
1
Continuation Phase
Protocol Violation
1
Continuation Phase
Adverse Event
1
Continuation Phase
Sponsor Concluded Study
1

Baseline Characteristics

There was no quantifiable retrospective data to report for this table.

Baseline characteristics by cohort

Baseline characteristics by cohort
Measure
APVO101 Prophylaxis - Safety Population
n=21 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Age, Customized
Age Group: < 6
10 Participants
n=21 Participants
Age, Customized
Age Group: 6 to < 12
11 Participants
n=21 Participants
Sex: Female, Male
Female
0 Participants
n=21 Participants
Sex: Female, Male
Male
21 Participants
n=21 Participants
Race (NIH/OMB)
American Indian or Alaska Native
0 Participants
n=21 Participants
Race (NIH/OMB)
Asian
0 Participants
n=21 Participants
Race (NIH/OMB)
Native Hawaiian or Other Pacific Islander
0 Participants
n=21 Participants
Race (NIH/OMB)
Black or African American
3 Participants
n=21 Participants
Race (NIH/OMB)
White
18 Participants
n=21 Participants
Race (NIH/OMB)
More than one race
0 Participants
n=21 Participants
Race (NIH/OMB)
Unknown or Not Reported
0 Participants
n=21 Participants
Region of Enrollment
Turkey
4 Participants
n=21 Participants
Region of Enrollment
Ukraine
8 Participants
n=21 Participants
Region of Enrollment
Brazil
3 Participants
n=21 Participants
Region of Enrollment
South Africa
3 Participants
n=21 Participants
Region of Enrollment
Moldova
1 Participants
n=21 Participants
Region of Enrollment
Georgia
2 Participants
n=21 Participants

PRIMARY outcome

Timeframe: Exposure Day 1 up to 50 exposure days (approximately 6 months)

Population: Analysis population included all participants for whom a legally acceptable representative had signed the informed consent/assent form and received at least one dose of APVO101.

The primary efficacy variable was the ABR while on prophylaxis to prevent bleeding episodes. The ABR was defined as the number of bleeding episodes per year.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=21 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Annualized Bleeding Rate (ABR)
2.93 bleeding episodes per year
Standard Deviation 4.59

PRIMARY outcome

Timeframe: Exposure Day 1 through study completion (up to 2.5 years)

Population: Analysis population included all participants for whom a legally acceptable representative had signed the informed consent/assent form and received at least one dose of APVO101.

The primary efficacy variable was the ABR while on prophylaxis to prevent bleeding episodes. The ABR was defined as the number of bleeding episodes per year.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=21 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Annualized Bleeding Rate (ABR) Overall
2.34 bleeding episodes per year
Standard Deviation 4.23

SECONDARY outcome

Timeframe: Pre-infusion to 50 hours post-infusion

Population: Analysis population included all participants for whom legally acceptable representative had signed informed consent/assent form, were in non-bleeding state, participated in single PK assessment at start of study and for whom an adequate PK profile had been obtained. "Number analyzed" signifies participants evaluable at specified time points.

Maximum post-infusion plasma concentration of FIX activity was measured at the following time points post infusion: 15-30 minutes, 4-6 hours, 24-26 hours and 46-50 hours.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=20 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Concentration (Cmax)
60.1 IU/dL
Standard Deviation 12.2

SECONDARY outcome

Timeframe: Pre-infusion to 50 hours post-infusion

Population: Analysis population included all participants for whom legally acceptable representative had signed informed consent/assent form, were in non-bleeding state, participated in single PK assessment at start of study and for whom an adequate PK profile had been obtained. "Number analyzed" signifies participants evaluable at specified time points.

Area under plasma concentration curve, FIX activity-time profile from time zero extrapolated to infinity. FIX activity was measured at the following time points post infusion: 15-30 minutes, 4-6 hours, 24-26 hours and 46-50 hours.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=21 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Area Under the Curve (0-inf)
1170 IU/dL/hr
Standard Deviation 231

SECONDARY outcome

Timeframe: Pre-infusion to 50 hours post-infusion

Population: Analysis population included all participants for whom legally acceptable representative had signed informed consent/assent form, were in non-bleeding state, participated in single PK assessment at start of study and for whom an adequate PK profile had been obtained. "Number analyzed" signifies participants evaluable at specified time points.

MRT is the average time the molecules of drug reside in the body before elimination.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=11 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Mean Residence Time (MRT)
20 hours
Standard Deviation 2.53

SECONDARY outcome

Timeframe: Pre-infusion to 50 hours post-infusion

Population: Analysis population included all participants for whom legally acceptable representative had signed informed consent/assent form, were in non-bleeding state, participated in single PK assessment at start of study and for whom an adequate PK profile had been obtained. "Number analyzed" signifies participants evaluable at specified time points.

Terminal half-life is the length of time required for the concentration of drug to decrease by one half of its starting dose in the body. FIX activity was measured at the following time points post infusion: 15-30 minutes, 4-6 hours, 24-26 hours and 46-50 hours.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=12 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Terminal Half-Life (t 1/2)
16.3 hours
Standard Deviation 2.2

SECONDARY outcome

Timeframe: Pre-infusion to 50 hours post-infusion

Population: Analysis population included all participants for whom legally acceptable representative had signed informed consent/assent form, were in non-bleeding state, participated in single PK assessment at start of study and for whom an adequate PK profile had been obtained. "Number analyzed" signifies participants evaluable at specified time points.

Clearance is a measure of the volume of plasma from which FIX activity is removed per unit time. Weight normalized clearance calculated as CL=Dose/AUC 0-inf. FIX activity was measured at the following time points post infusion: 15-30 minutes, 4-6 hours, 24-26 hours and 46-50 hours.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=11 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Clearance (CL)
6.8 mL/(kg*hr)
Standard Deviation 1.5

SECONDARY outcome

Timeframe: Pre-infusion to 50 hours post-infusion

Population: Analysis population included all participants for whom legally acceptable representative had signed informed consent/assent form, were in non-bleeding state, participated in single PK assessment at start of study and for whom an adequate PK profile had been obtained. "Number analyzed" signifies participants evaluable at specified time points.

Volume of distribution is defined as the theoretical volume in which the total amount of FIX would need to be uniformly distributed to produce the observed plasma concentration of FIX. Steady state volume of distribution (Vdss) is the apparent volume of distribution at steady-state. FIX activity was measured at the following time points post infusion: 15-30 minutes, 4-6 hours, 24-26 hours and 46-50 hours.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=11 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Volume of Distribution at Steady-State (Vdss)
134 mL/kg
Standard Deviation 30.6

SECONDARY outcome

Timeframe: Pre-infusion to 50 hours post-infusion

Population: Analysis population included all participants for whom legally acceptable representative had signed informed consent/assent form, were in non-bleeding state, participated in single PK assessment at start of study and for whom an adequate PK profile had been obtained. "Number analyzed" signifies participants evaluable at specified time points.

Incremental recovery was the increase in circulating FIX activity for every international unit (IU) of APVO101 administered per kilogram of body weight of participant. FIX activity was measured at the following time points post infusion: 15-30 minutes, 4-6 hours, 24-26 hours and 46-50 hours.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=20 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Incremental Recovery (IR)
0.790 IU/dL per IU/kg
Standard Deviation 0.156

SECONDARY outcome

Timeframe: Exposure Day 1 up to 50 exposure days (approximately 6 months)

Population: Analysis population included all participants for whom a legally acceptable representative had signed the informed consent/assent form, received at least one dose of APVO101 and who had experienced at least one bleeding episode.

Subjects rated APVO101 efficacy for each bleeding episode based on a four-point scale: 1. Excellent: a dramatic response with abrupt pain relief and clear reduction in joint or hemorrhage site size 2. Good: pain relief or reduction in hemorrhage site size that may have required an additional infusion for resolution; 3. Fair: probable or slight beneficial response usually requiring one of more additional infusions for resolution; 4. Poor: no improvement or condition worsens.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=24 bleeding episodes
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Subject Rating of APVO101 Efficacy - Evaluated at the Bleeding Episode Level (Treatment Phase)
Excellent
10 bleeding episodes
Subject Rating of APVO101 Efficacy - Evaluated at the Bleeding Episode Level (Treatment Phase)
Good
5 bleeding episodes
Subject Rating of APVO101 Efficacy - Evaluated at the Bleeding Episode Level (Treatment Phase)
Fair
0.0 bleeding episodes
Subject Rating of APVO101 Efficacy - Evaluated at the Bleeding Episode Level (Treatment Phase)
No infusions required to treat bleeding episode
7 bleeding episodes
Subject Rating of APVO101 Efficacy - Evaluated at the Bleeding Episode Level (Treatment Phase)
Missing
2 bleeding episodes
Subject Rating of APVO101 Efficacy - Evaluated at the Bleeding Episode Level (Treatment Phase)
Poor
0.0 bleeding episodes

SECONDARY outcome

Timeframe: Exposure Day 1 through study completion (up to 2.5 years)

Population: Analysis population included all participants for whom a legally acceptable representative had signed the informed consent/assent form, received at least one dose of APVO101 and who had experienced at least one bleeding episode.

Subjects rated APVO101 efficacy for each bleeding episode based on a four-point scale: 1. Excellent: a dramatic response with abrupt pain relief and clear reduction in joint or hemorrhage site size 2. Good: pain relief or reduction in hemorrhage site size that may have required an additional infusion for resolution; 3. Fair: probable or slight beneficial response usually requiring one of more additional infusions for resolution; 4. Poor: no improvement or condition worsens.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=52 bleeding episodes
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Subject Rating of APVO101 Efficacy - Evaluated at the Bleeding Episode Level (Overall)
Excellent
28 bleeding episodes
Subject Rating of APVO101 Efficacy - Evaluated at the Bleeding Episode Level (Overall)
Good
13 bleeding episodes
Subject Rating of APVO101 Efficacy - Evaluated at the Bleeding Episode Level (Overall)
Fair
0.0 bleeding episodes
Subject Rating of APVO101 Efficacy - Evaluated at the Bleeding Episode Level (Overall)
Poor
0.0 bleeding episodes
Subject Rating of APVO101 Efficacy - Evaluated at the Bleeding Episode Level (Overall)
No infusions required to treat bleeding episode
9 bleeding episodes
Subject Rating of APVO101 Efficacy - Evaluated at the Bleeding Episode Level (Overall)
Missing
2 bleeding episodes

SECONDARY outcome

Timeframe: Exposure Day 1 up to 50 exposure days (approximately 6 months)

Population: Analysis population included all participants for whom a legally acceptable representative had signed the informed consent/assent form and had received at least one dose of APVO101.

The investigator will indicate the overall assessment of APVO101 prophylaxis efficacy, considering the absence of bleeding episodes, site, severity and types of bleeding episodes treated, and other factors that might influence the therapeutic response. The investigator's efficacy assessment categories for prophylaxis will include: 'effective', 'partially effective' and 'not effective'.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=81 prophylactic efficacy assessment
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Investigator Rating of APVO101 Prophylaxis Efficacy (Treatment Phase)
Effective
80 prophylactic efficacy assessment
Investigator Rating of APVO101 Prophylaxis Efficacy (Treatment Phase)
Partially Effective
1 prophylactic efficacy assessment
Investigator Rating of APVO101 Prophylaxis Efficacy (Treatment Phase)
Not Effective
0 prophylactic efficacy assessment

SECONDARY outcome

Timeframe: Exposure Day 1 through study completion (up to 2.5 years)

Population: Analysis population included all participants for whom a legally acceptable representative had signed the informed consent/assent form and had received at least one dose of APVO101.

The investigator will indicate the overall assessment of APVO101 prophylaxis efficacy, considering the absence of bleeding episodes, site, severity and types of bleeding episodes treated, and other factors that might influence the therapeutic response. The investigator's efficacy assessment categories for prophylaxis will include: 'effective', 'partially effective' and 'not effective'.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=170 prophylactic efficacy assessment
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Investigator Rating of APVO101 Prophylaxis Efficacy (Overall)
Not Effective
0 prophylactic efficacy assessment
Investigator Rating of APVO101 Prophylaxis Efficacy (Overall)
Effective
167 prophylactic efficacy assessment
Investigator Rating of APVO101 Prophylaxis Efficacy (Overall)
Partially Effective
3 prophylactic efficacy assessment

SECONDARY outcome

Timeframe: Exposure Day 1 up to 50 exposure days (approximately 6 months)

Population: Analysis population included all participants for whom a legally acceptable representative had signed the informed consent/assent form, received at least one dose of APVO101 and who had experienced at least one bleeding episode.

Of the bleeding episodes requiring treatment, the investigator considered the site, severity and type of the bleeding episode while evaluating efficacy for control and management of the bleeding episode. The investigator's efficacy assessment categories control of bleeding episodes included: 'effective', 'partially effective' and 'not effective'.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=16 efficacy for control of bleeding episode
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Investigator Rating of APVO101 Efficacy for Control and Management of Bleeding Episodes (Treatment Phase)
Not effective
0 efficacy for control of bleeding episode
Investigator Rating of APVO101 Efficacy for Control and Management of Bleeding Episodes (Treatment Phase)
Effective
16 efficacy for control of bleeding episode
Investigator Rating of APVO101 Efficacy for Control and Management of Bleeding Episodes (Treatment Phase)
Partially effective
0 efficacy for control of bleeding episode

SECONDARY outcome

Timeframe: Exposure Day 1 through study completion (up to 2.5 years)

Population: Analysis population included all participants for whom a legally acceptable representative had signed the informed consent/assent form, received at least one dose of APVO101 and who had experienced at least one bleeding episode.

Of the bleeding episodes requiring treatment, the investigator considered the site, severity and type of the bleeding episode while evaluating efficacy for control and management of the bleeding episode. The investigator's efficacy assessment categories control of bleeding episodes included: 'effective', 'partially effective' and 'not effective'.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=35 efficacy for control of bleeding episode
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Investigator Rating of APVO101 Efficacy for Control and Management of Bleeding Episodes (Overall)
Effective
35 efficacy for control of bleeding episode
Investigator Rating of APVO101 Efficacy for Control and Management of Bleeding Episodes (Overall)
Not effective
0 efficacy for control of bleeding episode
Investigator Rating of APVO101 Efficacy for Control and Management of Bleeding Episodes (Overall)
Partially effective
0 efficacy for control of bleeding episode

OTHER_PRE_SPECIFIED outcome

Timeframe: Exposure Day 1 up to 50 exposure days (approximately 6 months)

Population: Analysis population included all participants for whom a legally acceptable representative had signed the informed consent/assent form and received at least one dose of APVO101.

Includes annualized bleeding rate for spontaneous bleeding (i.e. bleeds that occur without obvious cause).

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=21 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Spontaneous Annualized Bleeding Rate (Treatment Phase)
0.81 spontaneous bleeding episodes
Standard Deviation 1.93

OTHER_PRE_SPECIFIED outcome

Timeframe: Exposure Day 1 through study completion (up to 2.5 years)

Population: Analysis population included all participants for whom a legally acceptable representative had signed the informed consent/assent form and received at least one dose of APVO101.

Includes annualized bleeding rate for spontaneous bleeding (i.e. bleeds that occur without obvious cause).

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=21 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Spontaneous Annualized Bleeding Rate (Overall)
0.63 spontaneous bleeding episodes
Standard Deviation 1.26

OTHER_PRE_SPECIFIED outcome

Timeframe: Exposure Day 1 through study completion (up to 2.5 years)

Population: Analysis population included all participants for whom a legally acceptable representative had signed the informed consent/assent form and received at least one dose of APVO101.

Incidence of APVO101 immunogenicity response (development of inhibitory, non-inhibitory factor IX binding antibodies and incidence of antibodies to Chinese hamster ovary cell proteins \[CHOP\])

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=21 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Occurrence of Inhibitory Factor IX Antibodies (Overall)
0 Participants

OTHER_PRE_SPECIFIED outcome

Timeframe: Exposure Day 1 through study completion (up to 2.5 years)

Population: Analysis population included all participants for whom a legally acceptable representative had signed the informed consent/assent form and received at least one dose of APVO101.

Incidence of APVO101 immunogenicity response (development of inhibitory, non-inhibitory factor IX binding antibodies and incidence of antibodies to Chinese hamster ovary cell proteins \[CHOP\])

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=21 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Occurrence of Non-Inhibitory Factor IX Antibodies (Overall)
3 Participants

OTHER_PRE_SPECIFIED outcome

Timeframe: Exposure Day 1 through study completion (up to 2.5 years)

Population: Analysis population included all participants for whom a legally acceptable representative had signed the informed consent/assent form and received at least one dose of APVO101.

Incidence of APVO101 immunogenicity response (development of inhibitory, non-inhibitory factor IX binding antibodies and incidence of antibodies to Chinese hamster ovary cell proteins \[CHOP\])

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=21 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
Change from Baseline in values during the prespecified collection timepoints
Occurrence of Anti-CHOP Antibodies (Overall)
3 Participants

OTHER_PRE_SPECIFIED outcome

Timeframe: Day 1 (pre-dose), 15-30 minutes, 4-6 hours and 24-26 hours post-infusion

Population: To accommodate blood volume limitations for participants less than 17 kg, no thrombogenicity assessments were performed during the PK Phase. Participants weighing 17 kg to 19 kg, the 4 to 6 hour post-infusion timepoint was not collected.

This study included testing of thrombogenic markers at the PK stage to evaluate for thrombotic risk.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=13 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
n=13 Participants
Change from Baseline in values during the prespecified collection timepoints
Thrombogenicity Assessment - D-Dimer
4 to 6 hours post-infusion
0.452 mg/L
Standard Deviation 0.2955
0.045 mg/L
Standard Deviation 0.2051
Thrombogenicity Assessment - D-Dimer
24 to 26 hours post-infusion
0.578 mg/L
Standard Deviation 0.2766
0.114 mg/L
Standard Deviation 0.2586
Thrombogenicity Assessment - D-Dimer
Day 1, pre-infusion
0.432 mg/L
Standard Deviation 0.2320
Thrombogenicity Assessment - D-Dimer
15 to 30 minutes post-infusion
0.422 mg/L
Standard Deviation 0.1999
0.006 mg/L
Standard Deviation 0.1071

OTHER_PRE_SPECIFIED outcome

Timeframe: Day 1 (pre-dose), 15-30 minutes, 4-6 hours and 24-26 hours post-infusion

Population: To accommodate blood volume limitations for participants less than 17 kg, no thrombogenicity assessments were performed during the PK Phase. Participants weighing 17 kg to 19 kg, the 4 to 6 hour post-infusion timepoint was not collected.

This study included testing of thrombogenic markers at the PK stage to evaluate for thrombotic risk.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=13 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
n=13 Participants
Change from Baseline in values during the prespecified collection timepoints
Thrombogenicity Assessment - Thrombin/Antithrombin (TAT) Complex
4 to 6 hours post-infusion
12.17 ug/L
Standard Deviation 15.986
6.63 ug/L
Standard Deviation 17.399
Thrombogenicity Assessment - Thrombin/Antithrombin (TAT) Complex
24 to 26 hours post-infusion
12.45 ug/L
Standard Deviation 16.459
6.78 ug/L
Standard Deviation 17.081
Thrombogenicity Assessment - Thrombin/Antithrombin (TAT) Complex
15 to 30 minutes post-infusion
17.92 ug/L
Standard Deviation 22.971
12.71 ug/L
Standard Deviation 24.252
Thrombogenicity Assessment - Thrombin/Antithrombin (TAT) Complex
Day 1, pre-infusion
5.92 ug/L
Standard Deviation 2.579

OTHER_PRE_SPECIFIED outcome

Timeframe: Day 1 (pre-dose), 15-30 minutes, 4-6 hours and 24-26 hours post-infusion

Population: To accommodate blood volume limitations for participants less than 17 kg, no thrombogenicity assessments were performed during the PK Phase. Participants weighing 17 kg to 19 kg, the 4 to 6 hour post-infusion timepoint was not collected.

This study included testing of thrombogenic markers at the PK stage to evaluate for thrombotic risk.

Outcome measures

Outcome measures
Measure
APVO101 - Safety Population
n=13 Participants
Following a four day washout period or three half-lives washout of a factor IX product with a prolonged half-life, all study participants entered the PK Phase. * PK Phase - PK evaluation consisted of administration of a single 75 (±5) IU/kg dose, followed by factor IX activity and safety assessments up to 50 hours post-infusion. * Treatment Phase - after completion of the PK Phase, participants (safety population) received APVO101 prophylaxis (starting prophylaxis dose was to be determined based on APVO101 recovery; ideally within the recommended dose range: 35 to 75 IU/kg, twice weekly or at a frequency determined as appropriate by the Investigator) for 50 exposure days (approximately 6 months). * Continuation Phase - participants could continue APVO101 prophylaxis (recommended dose range: 35 to 75 IU/kg, twice weekly) for an additional 50 or more exposure days (approximately 6 months).
Change From Baseline
n=13 Participants
Change from Baseline in values during the prespecified collection timepoints
Thrombogenicity Assessment - Prothrombin Fragment 1+2
Day 1, pre-infusion
99.9 pmol/L
Standard Deviation 41.59
Thrombogenicity Assessment - Prothrombin Fragment 1+2
15 to 30 minutes post-infusion
318.0 pmol/L
Standard Deviation 433.64
218.1 pmol/L
Standard Deviation 439.48
Thrombogenicity Assessment - Prothrombin Fragment 1+2
4 to 6 hours post-infusion
238.6 pmol/L
Standard Deviation 330.63
139.5 pmol/L
Standard Deviation 303.66
Thrombogenicity Assessment - Prothrombin Fragment 1+2
24 to 26 hours post-infusion
223.0 pmol/L
Standard Deviation 246.46
123.1 pmol/L
Standard Deviation 251.48

Adverse Events

APVO101 Prophylaxis - Safety Population

Serious events: 2 serious events
Other events: 16 other events
Deaths: 0 deaths

Serious adverse events

Serious adverse events
Measure
APVO101 Prophylaxis - Safety Population
n=21 participants at risk
All subjects in the Safety Population received study treatment.
Injury, poisoning and procedural complications
Spinal Compression Fracture
4.8%
1/21 • Number of events 1 • Adverse events were monitored after the first dose of APVO101 through study completion (up to 2.5 years) with a minimum follow-up period of 30 days.
Collection method: All adverse events were reported by investigators assessments and subjects and/or their parent or legal guardian. Any clinically significant changes (as determined by the investigator) in laboratory test results, vital signs or physical exam were captured as adverse events. Additionally, subjects and/or their parent or legal guardian recorded AEs in the subject diary and the information was reviewed by the investigator during each scheduled visit.
Renal and urinary disorders
Hematuria
4.8%
1/21 • Number of events 1 • Adverse events were monitored after the first dose of APVO101 through study completion (up to 2.5 years) with a minimum follow-up period of 30 days.
Collection method: All adverse events were reported by investigators assessments and subjects and/or their parent or legal guardian. Any clinically significant changes (as determined by the investigator) in laboratory test results, vital signs or physical exam were captured as adverse events. Additionally, subjects and/or their parent or legal guardian recorded AEs in the subject diary and the information was reviewed by the investigator during each scheduled visit.

Other adverse events

Other adverse events
Measure
APVO101 Prophylaxis - Safety Population
n=21 participants at risk
All subjects in the Safety Population received study treatment.
Infections and infestations
Bronchitis
57.1%
12/21 • Number of events 31 • Adverse events were monitored after the first dose of APVO101 through study completion (up to 2.5 years) with a minimum follow-up period of 30 days.
Collection method: All adverse events were reported by investigators assessments and subjects and/or their parent or legal guardian. Any clinically significant changes (as determined by the investigator) in laboratory test results, vital signs or physical exam were captured as adverse events. Additionally, subjects and/or their parent or legal guardian recorded AEs in the subject diary and the information was reviewed by the investigator during each scheduled visit.
Infections and infestations
Influenza
9.5%
2/21 • Number of events 2 • Adverse events were monitored after the first dose of APVO101 through study completion (up to 2.5 years) with a minimum follow-up period of 30 days.
Collection method: All adverse events were reported by investigators assessments and subjects and/or their parent or legal guardian. Any clinically significant changes (as determined by the investigator) in laboratory test results, vital signs or physical exam were captured as adverse events. Additionally, subjects and/or their parent or legal guardian recorded AEs in the subject diary and the information was reviewed by the investigator during each scheduled visit.
Infections and infestations
Nasopharyngitis
23.8%
5/21 • Number of events 7 • Adverse events were monitored after the first dose of APVO101 through study completion (up to 2.5 years) with a minimum follow-up period of 30 days.
Collection method: All adverse events were reported by investigators assessments and subjects and/or their parent or legal guardian. Any clinically significant changes (as determined by the investigator) in laboratory test results, vital signs or physical exam were captured as adverse events. Additionally, subjects and/or their parent or legal guardian recorded AEs in the subject diary and the information was reviewed by the investigator during each scheduled visit.
Infections and infestations
Respiratory tract infection
9.5%
2/21 • Number of events 4 • Adverse events were monitored after the first dose of APVO101 through study completion (up to 2.5 years) with a minimum follow-up period of 30 days.
Collection method: All adverse events were reported by investigators assessments and subjects and/or their parent or legal guardian. Any clinically significant changes (as determined by the investigator) in laboratory test results, vital signs or physical exam were captured as adverse events. Additionally, subjects and/or their parent or legal guardian recorded AEs in the subject diary and the information was reviewed by the investigator during each scheduled visit.
Infections and infestations
Respiratory tract infection viral
9.5%
2/21 • Number of events 2 • Adverse events were monitored after the first dose of APVO101 through study completion (up to 2.5 years) with a minimum follow-up period of 30 days.
Collection method: All adverse events were reported by investigators assessments and subjects and/or their parent or legal guardian. Any clinically significant changes (as determined by the investigator) in laboratory test results, vital signs or physical exam were captured as adverse events. Additionally, subjects and/or their parent or legal guardian recorded AEs in the subject diary and the information was reviewed by the investigator during each scheduled visit.
Respiratory, thoracic and mediastinal disorders
Oropharyngeal Pain
9.5%
2/21 • Number of events 2 • Adverse events were monitored after the first dose of APVO101 through study completion (up to 2.5 years) with a minimum follow-up period of 30 days.
Collection method: All adverse events were reported by investigators assessments and subjects and/or their parent or legal guardian. Any clinically significant changes (as determined by the investigator) in laboratory test results, vital signs or physical exam were captured as adverse events. Additionally, subjects and/or their parent or legal guardian recorded AEs in the subject diary and the information was reviewed by the investigator during each scheduled visit.
Respiratory, thoracic and mediastinal disorders
Rhinorrhoea
9.5%
2/21 • Number of events 3 • Adverse events were monitored after the first dose of APVO101 through study completion (up to 2.5 years) with a minimum follow-up period of 30 days.
Collection method: All adverse events were reported by investigators assessments and subjects and/or their parent or legal guardian. Any clinically significant changes (as determined by the investigator) in laboratory test results, vital signs or physical exam were captured as adverse events. Additionally, subjects and/or their parent or legal guardian recorded AEs in the subject diary and the information was reviewed by the investigator during each scheduled visit.

Additional Information

Julissa Leon

Medexus Pharma

Phone: 3125483125

Results disclosure agreements

  • Principal investigator is a sponsor employee
  • Publication restrictions are in place