Trial Outcomes & Findings for Effect of Increasing Doses of Tiopronin on Cystine Capacity in Patients With Cystinuria (NCT NCT03663855)

NCT ID: NCT03663855

Last Updated: 2021-12-17

Results Overview

This measure reflects the ability of urine to take up more cystine

Recruitment status

COMPLETED

Study phase

PHASE2

Target enrollment

10 participants

Primary outcome timeframe

Baseline; Day 7

Results posted on

2021-12-17

Participant Flow

Multiple efforts to contact the PI/study team for the relevant data have failed. Therefore, per sequence data are not available to be reported for this assessment.

Participant milestones

Participant milestones
Measure
Cystinuria Patients
Phase 1: No medication, Phase 2: 500mg PO daily x 7 days (total 500mg), Phase 3: 500mg PO BID x 7 days (total 1g), Phase 4: 1g PO BID x 7 days (total 2g)
Overall Study
STARTED
10
Overall Study
COMPLETED
10
Overall Study
NOT COMPLETED
0

Reasons for withdrawal

Withdrawal data not reported

Baseline Characteristics

Effect of Increasing Doses of Tiopronin on Cystine Capacity in Patients With Cystinuria

Baseline characteristics by cohort

Baseline characteristics by cohort
Measure
Cystinuria Patients
n=10 Participants
Phase 1: No medication, Phase 2: 500mg PO daily x 7 days (total 500mg), Phase 3: 500mg PO BID x 7 days (total 1g), Phase 4: 1g PO BID x 7 days (total 2g)
Age, Continuous
45.3 years
STANDARD_DEVIATION 15.42 • n=5 Participants
Sex: Female, Male
Female
5 Participants
n=5 Participants
Sex: Female, Male
Male
5 Participants
n=5 Participants
Race (NIH/OMB)
American Indian or Alaska Native
0 Participants
n=5 Participants
Race (NIH/OMB)
Asian
1 Participants
n=5 Participants
Race (NIH/OMB)
Native Hawaiian or Other Pacific Islander
0 Participants
n=5 Participants
Race (NIH/OMB)
Black or African American
0 Participants
n=5 Participants
Race (NIH/OMB)
White
9 Participants
n=5 Participants
Race (NIH/OMB)
More than one race
0 Participants
n=5 Participants
Race (NIH/OMB)
Unknown or Not Reported
0 Participants
n=5 Participants
Region of Enrollment
United States
10 participants
n=5 Participants

PRIMARY outcome

Timeframe: Baseline; Day 7

This measure reflects the ability of urine to take up more cystine

Outcome measures

Outcome measures
Measure
Cystinuria Patients
n=10 Participants
Phase 1: No medication, Phase 2: 500mg PO daily x 7 days (total 500mg), Phase 3: 500mg PO BID x 7 days (total 1g), Phase 4: 1g PO BID x 7 days (total 2g)
Change in Cystine Capacity From Baseline
Phase 1
-63.6 mg/L
Standard Deviation 24.8
Change in Cystine Capacity From Baseline
Phase 2
76 mg/L
Standard Deviation 18.1
Change in Cystine Capacity From Baseline
Phase 3
53.4 mg/L
Standard Deviation 17.7
Change in Cystine Capacity From Baseline
Phase 4
103.1 mg/L
Standard Deviation 27.4

Adverse Events

Cystinuria Patients

Serious events: 0 serious events
Other events: 0 other events
Deaths: 0 deaths

Serious adverse events

Adverse event data not reported

Other adverse events

Adverse event data not reported

Additional Information

David Goldfarb, MD

NYU Langone Health

Phone: (212) 263-7300

Results disclosure agreements

  • Principal investigator is a sponsor employee
  • Publication restrictions are in place