Trial Outcomes & Findings for Bioequivalence of Orfadin 20 mg Compared to Orfadin 10 mg Capsules. (NCT NCT01857362)

NCT ID: NCT01857362

Last Updated: 2021-10-12

Results Overview

Recruitment status

COMPLETED

Study phase

PHASE1

Target enrollment

12 participants

Primary outcome timeframe

Day 1 predose and at 15, 30, 45 minutes and 1, 1.5, 2, 2.5, 3, 3.5, 4, 6, 8, 10, 12, 24, 36, 48 and 72 hours postdose

Results posted on

2021-10-12

Participant Flow

Participant milestones

Participant milestones
Measure
Nitisinone 1 x 20 mg, Then Nitisinone 2 x 10 mg
Participants first received one nitisinone capsule of 20 mg. After washout of 3 weeks participants then received two nitisinone capsules of 10 mg.
Nitisinone 2 x 10 mg, Then Nitisinone 1 x 20 mg
Participants first received two nitisinone capsules of 10 mg. After washout of 3 weeks participants then received one nitisinone capsule of 20 mg.
Overall Study
STARTED
6
6
Overall Study
COMPLETED
6
6
Overall Study
NOT COMPLETED
0
0

Reasons for withdrawal

Withdrawal data not reported

Baseline Characteristics

Bioequivalence of Orfadin 20 mg Compared to Orfadin 10 mg Capsules.

Baseline characteristics by cohort

Baseline characteristics by cohort
Measure
Overall Study
n=12 Participants
All treatment arms
Age, Continuous
31 years
STANDARD_DEVIATION 11 • n=5 Participants
Age, Categorical
<=18 years
0 Participants
n=5 Participants
Age, Categorical
Between 18 and 65 years
12 Participants
n=5 Participants
Age, Categorical
>=65 years
0 Participants
n=5 Participants
Sex: Female, Male
Female
3 Participants
n=5 Participants
Sex: Female, Male
Male
9 Participants
n=5 Participants
Region of Enrollment
Netherlands
12 participants
n=5 Participants

PRIMARY outcome

Timeframe: Day 1 predose and at 15, 30, 45 minutes and 1, 1.5, 2, 2.5, 3, 3.5, 4, 6, 8, 10, 12, 24, 36, 48 and 72 hours postdose

Population: Full analysis set was used; subjects with available PK data for at least one of the treatments.

Outcome measures

Outcome measures
Measure
Nitisinone 2 x 10 mg Capsules
n=12 Participants
Nitisinone 2 x 10 mg capsules
Nitisinone 1 x 20 mg Capsules
n=12 Participants
Nitisinone 1 x 20 mg capsules
The Area Under the Serum Concentration vs. Time Profile During 72 Hours After Dose (AUC72h).
262 uM*h
Interval 209.0 to 336.0
267 uM*h
Interval 210.0 to 341.0

PRIMARY outcome

Timeframe: Day 1 predose and at 15, 30, 45 minutes and 1, 1.5, 2, 2.5, 3, 3.5, 4, 6, 8, 10, 12, 24, 36, 48 and 72 hours postdose

Population: Full analysis set was used; subjects with available PK data for at least one of the treatments.

Outcome measures

Outcome measures
Measure
Nitisinone 2 x 10 mg Capsules
n=12 Participants
Nitisinone 2 x 10 mg capsules
Nitisinone 1 x 20 mg Capsules
n=12 Participants
Nitisinone 1 x 20 mg capsules
The Maximum Serum Concentration (Cmax).
6438 nM
Interval 4510.0 to 8950.0
6366 nM
Interval 4690.0 to 9330.0

Adverse Events

Nitisinone 2 x 10 mg Capsules

Serious events: 0 serious events
Other events: 4 other events
Deaths: 0 deaths

Nitisinone 1 x 20 mg Capsules

Serious events: 0 serious events
Other events: 4 other events
Deaths: 0 deaths

Serious adverse events

Adverse event data not reported

Other adverse events

Other adverse events
Measure
Nitisinone 2 x 10 mg Capsules
n=12 participants at risk
Nitisinone 2 x 10 mg capsules
Nitisinone 1 x 20 mg Capsules
n=12 participants at risk
Nitisinone 1 x 20 mg capsules
Gastrointestinal disorders
Abdominal pain
8.3%
1/12 • Number of events 1
0.00%
0/12
General disorders
Catheter site related reaction
0.00%
0/12
8.3%
1/12 • Number of events 1
General disorders
Hunger
0.00%
0/12
8.3%
1/12 • Number of events 1
Infections and infestations
Nasopharyngitis
0.00%
0/12
8.3%
1/12 • Number of events 1
Metabolism and nutrition disorders
Decreased appetite
8.3%
1/12 • Number of events 1
0.00%
0/12
Metabolism and nutrition disorders
Increased appetite
8.3%
1/12 • Number of events 1
0.00%
0/12
Nervous system disorders
Dizziness
0.00%
0/12
16.7%
2/12 • Number of events 2
Nervous system disorders
Headache
8.3%
1/12 • Number of events 1
16.7%
2/12 • Number of events 2
Nervous system disorders
Somnolence
8.3%
1/12 • Number of events 1
0.00%
0/12
Respiratory, thoracic and mediastinal disorders
Oropharyngeal pain
0.00%
0/12
8.3%
1/12 • Number of events 1
Skin and subcutaneous tissue disorders
Hyperhidrosis
0.00%
0/12
8.3%
1/12 • Number of events 1

Additional Information

Dr Erik Brouwer, Medical Director

Swedish Orphan Biovitrum

Phone: +4686972000

Results disclosure agreements

  • Principal investigator is a sponsor employee
  • Publication restrictions are in place

Restriction type: GT60