Trial Outcomes & Findings for Adenosine 2A Agonist Lexiscan in Children and Adults With Sickle Cell Disease (NCT NCT01085201)

NCT ID: NCT01085201

Last Updated: 2014-03-07

Results Overview

Per protocol, Lexiscan was considered "safe" if well tolerated based on number of DLTs reported. Stage 1 of the study was a 3+3 dose escalation study. Three doses were tested: 0.24 mcg/kg/hr (dose level 0), 0.6 mcg/kg/hr (dose level 1), and 1.44 mcg/kg/hr (dose level 2). Dose escalation continued until 6 participants were treated at the maximum planned dose (dose level 2). We studied a total of 15 patients in Stage 1. In Stages 2 and 3, if at least 2/3 participants tolerated the dose, an additional 3 participants were studied. We studied 6 participants in each of stages 2 and 3. In stage 2b, Lexiscan was studied for a longer (48 hr) duration in 3 participants. In stage 4, Lexiscan was studied in 3 pediatric participants.

Recruitment status

COMPLETED

Study phase

PHASE1

Target enrollment

39 participants

Primary outcome timeframe

30 to 54 hours plus 30-day follow-up

Results posted on

2014-03-07

Participant Flow

Recruitment began on 4/19/10 and ceased completely on 3/26/13. In Stages 1, 2 and 2b, patients were recruited from the medical clinic. For Stages 3 and 4, in which subjects were treated during a pain crisis hospitalization, patients were first informed about the study in clinic, and reminded about the study after being admitted.

Patients who were assigned to Stages 1, 2 or 2b, in which subjects were studied at baseline (i.e. not in pain crisis), could be excluded if they experienced a pain crisis in the interim period between enrollment and their scheduled study date.

Participant milestones

Participant milestones
Measure
Stage 1
12-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2
24-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2B
48-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 3
24-hour infusion to adults with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 4
24-hour infusion to children with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Overall Study
STARTED
18
7
5
6
3
Overall Study
COMPLETED
15
6
3
6
3
Overall Study
NOT COMPLETED
3
1
2
0
0

Reasons for withdrawal

Reasons for withdrawal
Measure
Stage 1
12-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2
24-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2B
48-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 3
24-hour infusion to adults with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 4
24-hour infusion to children with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Overall Study
Scheduling conflict
1
0
1
0
0
Overall Study
Unknown- no study drug
2
0
0
0
0
Overall Study
Fond ineligible after consent
0
1
1
0
0

Baseline Characteristics

Adenosine 2A Agonist Lexiscan in Children and Adults With Sickle Cell Disease

Baseline characteristics by cohort

Baseline characteristics by cohort
Measure
Stage 1
n=15 Participants
12-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2
n=6 Participants
24-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2B
n=3 Participants
48-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 3
n=6 Participants
24-hour infusion to adults with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 4
n=3 Participants
24-hour infusion to children with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Total
n=33 Participants
Total of all reporting groups
Age, Categorical
<=18 years
0 Participants
n=5 Participants
0 Participants
n=7 Participants
0 Participants
n=5 Participants
0 Participants
n=4 Participants
3 Participants
n=21 Participants
3 Participants
n=10 Participants
Age, Categorical
Between 18 and 65 years
15 Participants
n=5 Participants
6 Participants
n=7 Participants
3 Participants
n=5 Participants
6 Participants
n=4 Participants
0 Participants
n=21 Participants
30 Participants
n=10 Participants
Age, Categorical
>=65 years
0 Participants
n=5 Participants
0 Participants
n=7 Participants
0 Participants
n=5 Participants
0 Participants
n=4 Participants
0 Participants
n=21 Participants
0 Participants
n=10 Participants
Age, Continuous
33.71 years
STANDARD_DEVIATION 10.49 • n=5 Participants
33.84 years
STANDARD_DEVIATION 8.75 • n=7 Participants
23.68 years
STANDARD_DEVIATION 5.05 • n=5 Participants
31.61 years
STANDARD_DEVIATION 6.42 • n=4 Participants
16.77 years
STANDARD_DEVIATION 0.89 • n=21 Participants
30.9 years
STANDARD_DEVIATION 9.86 • n=10 Participants
Sex: Female, Male
Female
8 Participants
n=5 Participants
3 Participants
n=7 Participants
1 Participants
n=5 Participants
3 Participants
n=4 Participants
3 Participants
n=21 Participants
18 Participants
n=10 Participants
Sex: Female, Male
Male
7 Participants
n=5 Participants
3 Participants
n=7 Participants
2 Participants
n=5 Participants
3 Participants
n=4 Participants
0 Participants
n=21 Participants
15 Participants
n=10 Participants
Region of Enrollment
United States
15 participants
n=5 Participants
6 participants
n=7 Participants
3 participants
n=5 Participants
6 participants
n=4 Participants
3 participants
n=21 Participants
33 participants
n=10 Participants

PRIMARY outcome

Timeframe: 30 to 54 hours plus 30-day follow-up

Population: The number of participants was determined per protocol following a 3+3 design. In Stages 2b and 4, we received permission from the FDA, IRB, and DSMB to study only 3 subjects because we did not observe any prior DLT. One patient enrolled in Stage 2b withdrew consent during the infusion due to an unrelated toothache, and was excluded from analysis.

Per protocol, Lexiscan was considered "safe" if well tolerated based on number of DLTs reported. Stage 1 of the study was a 3+3 dose escalation study. Three doses were tested: 0.24 mcg/kg/hr (dose level 0), 0.6 mcg/kg/hr (dose level 1), and 1.44 mcg/kg/hr (dose level 2). Dose escalation continued until 6 participants were treated at the maximum planned dose (dose level 2). We studied a total of 15 patients in Stage 1. In Stages 2 and 3, if at least 2/3 participants tolerated the dose, an additional 3 participants were studied. We studied 6 participants in each of stages 2 and 3. In stage 2b, Lexiscan was studied for a longer (48 hr) duration in 3 participants. In stage 4, Lexiscan was studied in 3 pediatric participants.

Outcome measures

Outcome measures
Measure
Stage 1 - Dose Levels 0, 1 and 2
n=15 Participants
12-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2 - Dose Level 2
n=6 Participants
24-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2B - Dose Level 2
n=3 Participants
48-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 3 - Dose Level 2
n=6 Participants
24-hour infusion to adults with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 4 - Dose Level 2
n=3 Participants
24-hour infusion to children with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Dose Limiting Toxicities as a Measure of Whether Infusional Lexiscan is Safe in Individuals With SCD.
1 number of DLT
0 number of DLT
0 number of DLT
0 number of DLT
0 number of DLT

SECONDARY outcome

Timeframe: pre-drug to 54 hours

Population: The number of subjects was determined per protocol. Stage 1 was excluded as the goal was to determine the optimal markers for iNKT cells. Only 4 subjects were analyzed in Stage 2 because 24-hour samples were not obtained for 2 subjects. Stages 2b and 4 were not completely analyzed because these stages were completed early after studying 3 subjects.

Percentage of activated iNKT cells after receiving a 24-hour infusion of Lexiscan was compared to pre-drug. iNKT cell activation was evaluated using antibodies targeting the p65 subunit of nuclear factor-kappa B (phospho-NF-kB p65). Measures are given as percentage of change in phospho-NF-kB p65 activation in iNKT cells compared to pre-drug after a 24-hour infusion. iNKT cell activation in Stages 1, 2b, and 4 was not analyzed (see analysis population description).

Outcome measures

Outcome measures
Measure
Stage 1 - Dose Levels 0, 1 and 2
12-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2 - Dose Level 2
n=4 Participants
24-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2B - Dose Level 2
48-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 3 - Dose Level 2
n=6 Participants
24-hour infusion to adults with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 4 - Dose Level 2
24-hour infusion to children with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Percentage of Activated iNKT Cells and/or Activation Markers on iNKT Cells in Individuals With SCD.
-3 percentage of change in activation
Standard Deviation 0.30
-48 percentage of change in activation
Standard Deviation 0.30

SECONDARY outcome

Timeframe: pre-drug to 54 hours

Population: The number of participants was determined per protocol following a 3+3 design. Stages 1, 2 and 2b were excluded because this outcome measure is specific to the experience of a vaso-occlusive event, which was studied in Stages 3 and 4.

Pain was measured using a standardized pain scale. The scale is a 10-cm visual analogue scale (10 cm-long line printed on white paper), where 0 is no pain and 10 is maximum pain. Participants were asked to indicate their pain level by marking on the line prior to each blood draw.

Outcome measures

Outcome measures
Measure
Stage 1 - Dose Levels 0, 1 and 2
12-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2 - Dose Level 2
24-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2B - Dose Level 2
48-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 3 - Dose Level 2
n=6 Participants
24-hour infusion to adults with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 4 - Dose Level 2
n=3 Participants
24-hour infusion to children with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Pain Levels During a Vaso-occlusive Event in Children and Adults With SCD.
5.8 units on a scale
Standard Deviation 0.8
7.8 units on a scale
Standard Deviation 1.1

Adverse Events

Stage 1 - Dose Levels 0, 1 and 2

Serious events: 0 serious events
Other events: 0 other events
Deaths: 0 deaths

Stage 2 - Dose Level 2

Serious events: 2 serious events
Other events: 0 other events
Deaths: 0 deaths

Stage 2B - Dose Level 2

Serious events: 0 serious events
Other events: 0 other events
Deaths: 0 deaths

Stage 3 - Dose Level 2

Serious events: 1 serious events
Other events: 0 other events
Deaths: 0 deaths

Stage 4 - Dose Level 2

Serious events: 0 serious events
Other events: 0 other events
Deaths: 0 deaths

Serious adverse events

Serious adverse events
Measure
Stage 1 - Dose Levels 0, 1 and 2
n=15 participants at risk
12-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2 - Dose Level 2
n=6 participants at risk
24-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 2B - Dose Level 2
n=3 participants at risk
48-hour infusion to adults with SCD who are not having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 3 - Dose Level 2
n=6 participants at risk
24-hour infusion to adults with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AND CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Stage 4 - Dose Level 2
n=3 participants at risk
24-hour infusion to children with SCD who are having a pain crisis. THIS STAGE IS COMPLETE AFTER STUDYING 3 PATIENTS BY AGREEMENT FROM THE FDA, IRB, AND DSMB. THIS STAGE IS CLOSED TO ACCRUAL. Lexiscan : Given as an infusion
Blood and lymphatic system disorders
Sickle cell crisis with prolonged hospitalization - Grade 2
0.00%
0/15 • 3 years
16.7%
1/6 • Number of events 1 • 3 years
0.00%
0/3 • 3 years
0.00%
0/6 • 3 years
0.00%
0/3 • 3 years
Blood and lymphatic system disorders
Uncomplicated vaso-occlusive crisis requiring hospitalization - Grade 3
0.00%
0/15 • 3 years
16.7%
1/6 • Number of events 2 • 3 years
0.00%
0/3 • 3 years
16.7%
1/6 • Number of events 1 • 3 years
0.00%
0/3 • 3 years
Musculoskeletal and connective tissue disorders
Rib pain, leading to hospitalization - Grade 3
0.00%
0/15 • 3 years
0.00%
0/6 • 3 years
0.00%
0/3 • 3 years
16.7%
1/6 • Number of events 1 • 3 years
0.00%
0/3 • 3 years

Other adverse events

Adverse event data not reported

Additional Information

Dr. Joshua J. Field

BloodCenter of Wisconsin

Phone: 414-937-3848

Results disclosure agreements

  • Principal investigator is a sponsor employee
  • Publication restrictions are in place